Bilateral Recurrent Laryngeal Nerve Palsy following Total Thyroidectomy in Triple A Syndrome, an Unexpected but Critical Complication
Introduction. Triple “A” syndrome (TAS) is a rare autosomal recessive disorder that presents in childhood with achalasia cardia, alacrima, ACTH-resistant adrenal insufficiency, with sensorimotor and autonomic polyneuropathy developing later in the course of the disease. Case Presentation. An adult w...
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Wiley
2021-01-01
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| Series: | Case Reports in Otolaryngology |
| Online Access: | http://dx.doi.org/10.1155/2021/1315117 |
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| author | Mathieu Chamberland Marc-Antoine Poulin Danielle Beaudoin |
| author_facet | Mathieu Chamberland Marc-Antoine Poulin Danielle Beaudoin |
| author_sort | Mathieu Chamberland |
| collection | DOAJ |
| description | Introduction. Triple “A” syndrome (TAS) is a rare autosomal recessive disorder that presents in childhood with achalasia cardia, alacrima, ACTH-resistant adrenal insufficiency, with sensorimotor and autonomic polyneuropathy developing later in the course of the disease. Case Presentation. An adult white male affected by this syndrome underwent an uneventful total thyroidectomy for malignancy and suffered delayed bilateral recurrent laryngeal nerve palsy in the early postoperative hours. The palsy spontaneously resolved after a five-week course. Conclusion. Given the rarity of this severe condition and the absence of surgical or medical causes identifiable, there is possibility that it is the neurological involvement caused by TAS that predisposed the patient to this adverse outcome, precipitated by standard manipulations during surgery. |
| format | Article |
| id | doaj-art-7bd1e22ab22440a790c9e9d717f4fdf9 |
| institution | Kabale University |
| issn | 2090-6773 |
| language | English |
| publishDate | 2021-01-01 |
| publisher | Wiley |
| record_format | Article |
| series | Case Reports in Otolaryngology |
| spelling | doaj-art-7bd1e22ab22440a790c9e9d717f4fdf92025-02-03T06:06:33ZengWileyCase Reports in Otolaryngology2090-67732021-01-01202110.1155/2021/1315117Bilateral Recurrent Laryngeal Nerve Palsy following Total Thyroidectomy in Triple A Syndrome, an Unexpected but Critical ComplicationMathieu Chamberland0Marc-Antoine Poulin1Danielle Beaudoin2Hôpital de l’Enfant-JésusHôpital de l’Enfant-JésusHôpital de l’Enfant-JésusIntroduction. Triple “A” syndrome (TAS) is a rare autosomal recessive disorder that presents in childhood with achalasia cardia, alacrima, ACTH-resistant adrenal insufficiency, with sensorimotor and autonomic polyneuropathy developing later in the course of the disease. Case Presentation. An adult white male affected by this syndrome underwent an uneventful total thyroidectomy for malignancy and suffered delayed bilateral recurrent laryngeal nerve palsy in the early postoperative hours. The palsy spontaneously resolved after a five-week course. Conclusion. Given the rarity of this severe condition and the absence of surgical or medical causes identifiable, there is possibility that it is the neurological involvement caused by TAS that predisposed the patient to this adverse outcome, precipitated by standard manipulations during surgery.http://dx.doi.org/10.1155/2021/1315117 |
| spellingShingle | Mathieu Chamberland Marc-Antoine Poulin Danielle Beaudoin Bilateral Recurrent Laryngeal Nerve Palsy following Total Thyroidectomy in Triple A Syndrome, an Unexpected but Critical Complication Case Reports in Otolaryngology |
| title | Bilateral Recurrent Laryngeal Nerve Palsy following Total Thyroidectomy in Triple A Syndrome, an Unexpected but Critical Complication |
| title_full | Bilateral Recurrent Laryngeal Nerve Palsy following Total Thyroidectomy in Triple A Syndrome, an Unexpected but Critical Complication |
| title_fullStr | Bilateral Recurrent Laryngeal Nerve Palsy following Total Thyroidectomy in Triple A Syndrome, an Unexpected but Critical Complication |
| title_full_unstemmed | Bilateral Recurrent Laryngeal Nerve Palsy following Total Thyroidectomy in Triple A Syndrome, an Unexpected but Critical Complication |
| title_short | Bilateral Recurrent Laryngeal Nerve Palsy following Total Thyroidectomy in Triple A Syndrome, an Unexpected but Critical Complication |
| title_sort | bilateral recurrent laryngeal nerve palsy following total thyroidectomy in triple a syndrome an unexpected but critical complication |
| url | http://dx.doi.org/10.1155/2021/1315117 |
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