The phenotypic spectrum of the Cornelia de Lange‐like “Alazami‐Yuan syndrome”: A case report of the 7th diagnosed individual and review of the literature

Key Clinical Message We present a 17‐year‐old female with a childhood clinical diagnosis of Cornelia de Lange Syndrome (CdLS), however later genetic testing identified compound heterozygous variants in TAF6, consistent with AYS. This case report adds to the phenotypic spectrum observed in AYS, and d...

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Main Authors: Annie Pappas, Mary Mooney, Katherine Kohnen, Joshua W. Owens, Wenying Zhang, Robert J. Hopkin, Amelle Shillington
Format: Article
Language:English
Published: Wiley 2025-05-01
Series:Clinical Case Reports
Subjects:
Online Access:https://doi.org/10.1002/ccr3.9208
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author Annie Pappas
Mary Mooney
Katherine Kohnen
Joshua W. Owens
Wenying Zhang
Robert J. Hopkin
Amelle Shillington
author_facet Annie Pappas
Mary Mooney
Katherine Kohnen
Joshua W. Owens
Wenying Zhang
Robert J. Hopkin
Amelle Shillington
author_sort Annie Pappas
collection DOAJ
description Key Clinical Message We present a 17‐year‐old female with a childhood clinical diagnosis of Cornelia de Lange Syndrome (CdLS), however later genetic testing identified compound heterozygous variants in TAF6, consistent with AYS. This case report adds to the phenotypic spectrum observed in AYS, and draws connections to transcriptional pathways between CdLS and AYS.
format Article
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institution OA Journals
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language English
publishDate 2025-05-01
publisher Wiley
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series Clinical Case Reports
spelling doaj-art-1a88a07a86d843958248b64ccf99f1f92025-08-20T01:56:46ZengWileyClinical Case Reports2050-09042025-05-01135n/an/a10.1002/ccr3.9208The phenotypic spectrum of the Cornelia de Lange‐like “Alazami‐Yuan syndrome”: A case report of the 7th diagnosed individual and review of the literatureAnnie Pappas0Mary Mooney1Katherine Kohnen2Joshua W. Owens3Wenying Zhang4Robert J. Hopkin5Amelle Shillington6Department of Pediatrics University of Cincinnati College of Medicine Cincinnati Ohio USADepartment of Pediatrics University of Cincinnati College of Medicine Cincinnati Ohio USADepartment of Pediatrics University of Cincinnati College of Medicine Cincinnati Ohio USADivision of Human Genetics Cincinnati Children's Hospital Medical Center Cincinnati Ohio USADivision of Human Genetics Cincinnati Children's Hospital Medical Center Cincinnati Ohio USADivision of Human Genetics Cincinnati Children's Hospital Medical Center Cincinnati Ohio USADivision of Human Genetics Cincinnati Children's Hospital Medical Center Cincinnati Ohio USAKey Clinical Message We present a 17‐year‐old female with a childhood clinical diagnosis of Cornelia de Lange Syndrome (CdLS), however later genetic testing identified compound heterozygous variants in TAF6, consistent with AYS. This case report adds to the phenotypic spectrum observed in AYS, and draws connections to transcriptional pathways between CdLS and AYS.https://doi.org/10.1002/ccr3.9208Alazami‐Yuan syndromeCornelia de Lange‐like syndromeTAF6transcriptomopathies
spellingShingle Annie Pappas
Mary Mooney
Katherine Kohnen
Joshua W. Owens
Wenying Zhang
Robert J. Hopkin
Amelle Shillington
The phenotypic spectrum of the Cornelia de Lange‐like “Alazami‐Yuan syndrome”: A case report of the 7th diagnosed individual and review of the literature
Clinical Case Reports
Alazami‐Yuan syndrome
Cornelia de Lange‐like syndrome
TAF6
transcriptomopathies
title The phenotypic spectrum of the Cornelia de Lange‐like “Alazami‐Yuan syndrome”: A case report of the 7th diagnosed individual and review of the literature
title_full The phenotypic spectrum of the Cornelia de Lange‐like “Alazami‐Yuan syndrome”: A case report of the 7th diagnosed individual and review of the literature
title_fullStr The phenotypic spectrum of the Cornelia de Lange‐like “Alazami‐Yuan syndrome”: A case report of the 7th diagnosed individual and review of the literature
title_full_unstemmed The phenotypic spectrum of the Cornelia de Lange‐like “Alazami‐Yuan syndrome”: A case report of the 7th diagnosed individual and review of the literature
title_short The phenotypic spectrum of the Cornelia de Lange‐like “Alazami‐Yuan syndrome”: A case report of the 7th diagnosed individual and review of the literature
title_sort phenotypic spectrum of the cornelia de lange like alazami yuan syndrome a case report of the 7th diagnosed individual and review of the literature
topic Alazami‐Yuan syndrome
Cornelia de Lange‐like syndrome
TAF6
transcriptomopathies
url https://doi.org/10.1002/ccr3.9208
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