Very late relapse of Burkitt's lymphoma in an EBV-negative patient after 20 years of complete remission

Burkitt's lymphoma (BL) is an aggressive B-cell lymphoma that occurs in children and adults. It is a chemosensitive lymphoma with very exceptional cases of late relapse.We report the case of a 32-year-old male, originally from a nonendemic area for BL, who was successfully treated for abdominal...

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Main Authors: Kmar Mrad, Nader Slama, Nouha Ben Abdeljalil, Zaineb Mlayah, Wiem Boufrikha, Abdelfattah Zakhama, Sarra Boukhris, Mohamed Adnene Laatiri
Format: Article
Language:English
Published: Elsevier 2024-01-01
Series:Leukemia Research Reports
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Online Access:http://www.sciencedirect.com/science/article/pii/S2213048924000608
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author Kmar Mrad
Nader Slama
Nouha Ben Abdeljalil
Zaineb Mlayah
Wiem Boufrikha
Abdelfattah Zakhama
Sarra Boukhris
Mohamed Adnene Laatiri
author_facet Kmar Mrad
Nader Slama
Nouha Ben Abdeljalil
Zaineb Mlayah
Wiem Boufrikha
Abdelfattah Zakhama
Sarra Boukhris
Mohamed Adnene Laatiri
author_sort Kmar Mrad
collection DOAJ
description Burkitt's lymphoma (BL) is an aggressive B-cell lymphoma that occurs in children and adults. It is a chemosensitive lymphoma with very exceptional cases of late relapse.We report the case of a 32-year-old male, originally from a nonendemic area for BL, who was successfully treated for abdominal BL 20 years ago. He described a two-month history of cervical swelling and a one-week history of dyspnea. Physical examination was unremarkable except for a left submandibular mass that extended to the collarbone. An ultrasound of the neck revealed cervical lymphadenopathy. The patient was submitted to a lymph node biopsy with an immunohistochemical analysis, which concluded to the diagnosis of BL. Screening for recent Epstein-Barr-Virus (EBV) infection was negative. We considered this a very late relapse (VLR) of the original disease, and the patient was treated according to the same initial protocol. Unfortunately, he suffered a second relapse and died.We report an unusual case of a VLR of nonendemic BL in an EBV-negative patient, occurring 20 years after achieving complete remission following the initial chemotherapy.
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series Leukemia Research Reports
spelling doaj-art-fdeee5e9a6c84242af1a4f0a06b5dce52025-08-20T02:19:37ZengElsevierLeukemia Research Reports2213-04892024-01-012210047010.1016/j.lrr.2024.100470Very late relapse of Burkitt's lymphoma in an EBV-negative patient after 20 years of complete remissionKmar Mrad0Nader Slama1Nouha Ben Abdeljalil2Zaineb Mlayah3Wiem Boufrikha4Abdelfattah Zakhama5Sarra Boukhris6Mohamed Adnene Laatiri7Hematology Department, Fattouma Bourguiba University Hospital of Monastir, Avenue Farhat Hached, Monastir, 5000, Tunisia; Corresponding author at: Hematology Department, Fattouma Bourguiba University Hospital of Monastir, Avenue Farhat Hached, Monastir 5000, Tunisia.Hematology Department, Fattouma Bourguiba University Hospital of Monastir, Avenue Farhat Hached, Monastir, 5000, TunisiaPathology Department, Fattouma Bourguiba University Hospital of Monastir, Avenue Farhat Hached, Monastir, 5000, TunisiaHematology Department, Fattouma Bourguiba University Hospital of Monastir, Avenue Farhat Hached, Monastir, 5000, TunisiaHematology Department, Fattouma Bourguiba University Hospital of Monastir, Avenue Farhat Hached, Monastir, 5000, TunisiaPathology Department, Fattouma Bourguiba University Hospital of Monastir, Avenue Farhat Hached, Monastir, 5000, TunisiaHematology Department, Fattouma Bourguiba University Hospital of Monastir, Avenue Farhat Hached, Monastir, 5000, TunisiaHematology Department, Fattouma Bourguiba University Hospital of Monastir, Avenue Farhat Hached, Monastir, 5000, TunisiaBurkitt's lymphoma (BL) is an aggressive B-cell lymphoma that occurs in children and adults. It is a chemosensitive lymphoma with very exceptional cases of late relapse.We report the case of a 32-year-old male, originally from a nonendemic area for BL, who was successfully treated for abdominal BL 20 years ago. He described a two-month history of cervical swelling and a one-week history of dyspnea. Physical examination was unremarkable except for a left submandibular mass that extended to the collarbone. An ultrasound of the neck revealed cervical lymphadenopathy. The patient was submitted to a lymph node biopsy with an immunohistochemical analysis, which concluded to the diagnosis of BL. Screening for recent Epstein-Barr-Virus (EBV) infection was negative. We considered this a very late relapse (VLR) of the original disease, and the patient was treated according to the same initial protocol. Unfortunately, he suffered a second relapse and died.We report an unusual case of a VLR of nonendemic BL in an EBV-negative patient, occurring 20 years after achieving complete remission following the initial chemotherapy.http://www.sciencedirect.com/science/article/pii/S2213048924000608B-cell lymphomaBurkitt lymphomaChemotherapyRecurrence
spellingShingle Kmar Mrad
Nader Slama
Nouha Ben Abdeljalil
Zaineb Mlayah
Wiem Boufrikha
Abdelfattah Zakhama
Sarra Boukhris
Mohamed Adnene Laatiri
Very late relapse of Burkitt's lymphoma in an EBV-negative patient after 20 years of complete remission
Leukemia Research Reports
B-cell lymphoma
Burkitt lymphoma
Chemotherapy
Recurrence
title Very late relapse of Burkitt's lymphoma in an EBV-negative patient after 20 years of complete remission
title_full Very late relapse of Burkitt's lymphoma in an EBV-negative patient after 20 years of complete remission
title_fullStr Very late relapse of Burkitt's lymphoma in an EBV-negative patient after 20 years of complete remission
title_full_unstemmed Very late relapse of Burkitt's lymphoma in an EBV-negative patient after 20 years of complete remission
title_short Very late relapse of Burkitt's lymphoma in an EBV-negative patient after 20 years of complete remission
title_sort very late relapse of burkitt s lymphoma in an ebv negative patient after 20 years of complete remission
topic B-cell lymphoma
Burkitt lymphoma
Chemotherapy
Recurrence
url http://www.sciencedirect.com/science/article/pii/S2213048924000608
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