Seromucinous Hamartoma of the Lateral Nasal Wall with Infiltration of the Orbit: A Rare Case Report and Review of the Literature

Seromucinous hamartoma is a rare benign glandular proliferation arising from the respiratory epithelium of the sinonasal tract and nasopharynx. It was described for the first time in 1974 by Baillie and Batsakis. Since then, few cases have been reported in the literature with most of them occurring...

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Main Authors: Lentiona Basiari, Maria Michali, Ioannis Komnos, Georgios Tsirves, Victoria Tsoumani, Ioannis Kastanioudakis
Format: Article
Language:English
Published: Wiley 2023-01-01
Series:Case Reports in Otolaryngology
Online Access:http://dx.doi.org/10.1155/2023/1923015
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author Lentiona Basiari
Maria Michali
Ioannis Komnos
Georgios Tsirves
Victoria Tsoumani
Ioannis Kastanioudakis
author_facet Lentiona Basiari
Maria Michali
Ioannis Komnos
Georgios Tsirves
Victoria Tsoumani
Ioannis Kastanioudakis
author_sort Lentiona Basiari
collection DOAJ
description Seromucinous hamartoma is a rare benign glandular proliferation arising from the respiratory epithelium of the sinonasal tract and nasopharynx. It was described for the first time in 1974 by Baillie and Batsakis. Since then, few cases have been reported in the literature with most of them occurring in the posterior nasal septum. We report the case of a 52-year-old woman that presented to our department with left periorbital edema, pain, and dacryorrhea due to seromucinous hamartoma arising from the left inferior turbinate and extending through the lateral nasal wall into the maxilla, the nasolacrimal duct, and the orbit. Endoscopic medial maxillectomy and endoscopic transnasal orbital tumor resection were performed. The patient remains symptom-free for 16 months, till her most recent follow-up. Seromucinous hamartoma of the nasal cavity is an exceedingly rare diagnosis, especially in the lateral nasal wall. It should be included in the differential diagnosis of nasal tumors. According to the literature review, this is the first case report of seromucinous hamartoma with orbit infiltration. Endonasal endoscopic resection is the treatment of choice.
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spelling doaj-art-f7adc1ed84424796a8cdec338ccf3ea52025-02-03T05:44:34ZengWileyCase Reports in Otolaryngology2090-67732023-01-01202310.1155/2023/1923015Seromucinous Hamartoma of the Lateral Nasal Wall with Infiltration of the Orbit: A Rare Case Report and Review of the LiteratureLentiona Basiari0Maria Michali1Ioannis Komnos2Georgios Tsirves3Victoria Tsoumani4Ioannis Kastanioudakis5Department of Otorhinolaryngology-Head and Neck SurgeryDepartment of Otorhinolaryngology-Head and Neck SurgeryDepartment of Otorhinolaryngology-Head and Neck SurgeryDepartment of Otorhinolaryngology-Head and Neck SurgeryDepartment of Otorhinolaryngology-Head and Neck SurgeryDepartment of Otorhinolaryngology-Head and Neck SurgerySeromucinous hamartoma is a rare benign glandular proliferation arising from the respiratory epithelium of the sinonasal tract and nasopharynx. It was described for the first time in 1974 by Baillie and Batsakis. Since then, few cases have been reported in the literature with most of them occurring in the posterior nasal septum. We report the case of a 52-year-old woman that presented to our department with left periorbital edema, pain, and dacryorrhea due to seromucinous hamartoma arising from the left inferior turbinate and extending through the lateral nasal wall into the maxilla, the nasolacrimal duct, and the orbit. Endoscopic medial maxillectomy and endoscopic transnasal orbital tumor resection were performed. The patient remains symptom-free for 16 months, till her most recent follow-up. Seromucinous hamartoma of the nasal cavity is an exceedingly rare diagnosis, especially in the lateral nasal wall. It should be included in the differential diagnosis of nasal tumors. According to the literature review, this is the first case report of seromucinous hamartoma with orbit infiltration. Endonasal endoscopic resection is the treatment of choice.http://dx.doi.org/10.1155/2023/1923015
spellingShingle Lentiona Basiari
Maria Michali
Ioannis Komnos
Georgios Tsirves
Victoria Tsoumani
Ioannis Kastanioudakis
Seromucinous Hamartoma of the Lateral Nasal Wall with Infiltration of the Orbit: A Rare Case Report and Review of the Literature
Case Reports in Otolaryngology
title Seromucinous Hamartoma of the Lateral Nasal Wall with Infiltration of the Orbit: A Rare Case Report and Review of the Literature
title_full Seromucinous Hamartoma of the Lateral Nasal Wall with Infiltration of the Orbit: A Rare Case Report and Review of the Literature
title_fullStr Seromucinous Hamartoma of the Lateral Nasal Wall with Infiltration of the Orbit: A Rare Case Report and Review of the Literature
title_full_unstemmed Seromucinous Hamartoma of the Lateral Nasal Wall with Infiltration of the Orbit: A Rare Case Report and Review of the Literature
title_short Seromucinous Hamartoma of the Lateral Nasal Wall with Infiltration of the Orbit: A Rare Case Report and Review of the Literature
title_sort seromucinous hamartoma of the lateral nasal wall with infiltration of the orbit a rare case report and review of the literature
url http://dx.doi.org/10.1155/2023/1923015
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