Acrodermatitis Continua of Hallopeau and Generalised Pustular Psoriasis: Case Reports of Two Different Manifestations of IL36RN Mutation in Siblings

Mengjiao Gu,1,2,* Hanjing Huang,1,2,* Zhanshuo Xiao,3,* Fanzhang Meng,4 Han Sheng,4 Zhimin Lin,5 Chen Li,6,7 Yuanhao Wu1,2 1First Teaching Hospital of Tianjin University of Traditional Chinese Medicine, Tianjin, People’s Republic of China; 2National Clinical Research Center f...

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Main Authors: Gu M, Huang H, Xiao Z, Meng F, Sheng H, Lin Z, Li C, Wu Y
Format: Article
Language:English
Published: Dove Medical Press 2025-03-01
Series:Psoriasis: Targets and Therapy
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Online Access:https://www.dovepress.com/acrodermatitis-continua-of-hallopeau-and-generalised-pustular-psoriasi-peer-reviewed-fulltext-article-PTT
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author Gu M
Huang H
Xiao Z
Meng F
Sheng H
Lin Z
Li C
Wu Y
author_facet Gu M
Huang H
Xiao Z
Meng F
Sheng H
Lin Z
Li C
Wu Y
author_sort Gu M
collection DOAJ
description Mengjiao Gu,1,2,* Hanjing Huang,1,2,* Zhanshuo Xiao,3,* Fanzhang Meng,4 Han Sheng,4 Zhimin Lin,5 Chen Li,6,7 Yuanhao Wu1,2 1First Teaching Hospital of Tianjin University of Traditional Chinese Medicine, Tianjin, People’s Republic of China; 2National Clinical Research Center for Chinese Medicine Acupuncture and Moxibustion, Tianjin, People’s Republic of China; 3Department of Dermatology, Guang’anmen Hospital, China Academy of Chinese Medical Sciences, Beijing, People’s Republic of China; 4School of Clinical Medicine, Beijing University of Chinese Medicine, Beijing, People’s Republic of China; 5Third Affiliated Hospital, Beijing University of Chinese Medicine, Beijing, People’s Republic of China; 6Department of Rheumatology, Fangshan Hospital Beijing University of Chinese Medicine, Beijing, People’s Republic of China; 7Department of Dermatology, Tianjin Institute of Integrative Dermatology, Tianjin Academy of Traditional Chinese Medicine Affiliated Hospital, Tianjin, People’s Republic of China*These authors contributed equally to this workCorrespondence: Chen Li, Fangshan Hospital Beijing University of Chinese Medicine, Beijing, China; Tianjin Academy of Traditional Chinese Medicine Affiliated Hospital, Tianjin, People’s Republic of China, Tel +86 010 13810988688, Email casio1981@163.com Yuanhao Wu, First Teaching Hospital of Tianjin University of Traditional Chinese Medicine, Tianjin, People’s Republic of China, Tel +86 022 16622507882, Email doctor.wuyh@gmail.comAbstract: In our manuscript, we present a case study of siblings with Generalized Pustular Psoriasis (GPP) and Acrodermatitis Continua of Hallopeau (ACH), both harboring IL36RN gene mutations. The 3-year-old proband exhibited systemic pustules leading to a GPP diagnosis, while his 6-year-old sister developed nail ulcers and subungual pustules characteristic of ACH. Despite standard treatments, their conditions were refractory. Genetic analysis revealed a homozygous splice variant c.115+6 T>C, with heterozygous parents. This case underscores the role of IL36RN mutations in pustular psoriasis and supports ACH as a localized form of the disease. The distinct subtypes in siblings with identical mutations suggest a complex pathogenesis influenced by additional factors. Our findings highlight the importance of genetic testing in pustular psoriasis and warrant further investigation into the phenotypic variability of IL36RN-related disease.Keywords: Acrodermatitis Continua of Hallopeau, generalised pustular psoriasis, IL36RN gene mutations
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spelling doaj-art-e1defb01c8ff4a8eb97ab5923b0e89552025-08-20T01:49:59ZengDove Medical PressPsoriasis: Targets and Therapy2230-326X2025-03-01Volume 156770101520Acrodermatitis Continua of Hallopeau and Generalised Pustular Psoriasis: Case Reports of Two Different Manifestations of IL36RN Mutation in SiblingsGu MHuang HXiao ZMeng FSheng HLin ZLi CWu YMengjiao Gu,1,2,* Hanjing Huang,1,2,* Zhanshuo Xiao,3,* Fanzhang Meng,4 Han Sheng,4 Zhimin Lin,5 Chen Li,6,7 Yuanhao Wu1,2 1First Teaching Hospital of Tianjin University of Traditional Chinese Medicine, Tianjin, People’s Republic of China; 2National Clinical Research Center for Chinese Medicine Acupuncture and Moxibustion, Tianjin, People’s Republic of China; 3Department of Dermatology, Guang’anmen Hospital, China Academy of Chinese Medical Sciences, Beijing, People’s Republic of China; 4School of Clinical Medicine, Beijing University of Chinese Medicine, Beijing, People’s Republic of China; 5Third Affiliated Hospital, Beijing University of Chinese Medicine, Beijing, People’s Republic of China; 6Department of Rheumatology, Fangshan Hospital Beijing University of Chinese Medicine, Beijing, People’s Republic of China; 7Department of Dermatology, Tianjin Institute of Integrative Dermatology, Tianjin Academy of Traditional Chinese Medicine Affiliated Hospital, Tianjin, People’s Republic of China*These authors contributed equally to this workCorrespondence: Chen Li, Fangshan Hospital Beijing University of Chinese Medicine, Beijing, China; Tianjin Academy of Traditional Chinese Medicine Affiliated Hospital, Tianjin, People’s Republic of China, Tel +86 010 13810988688, Email casio1981@163.com Yuanhao Wu, First Teaching Hospital of Tianjin University of Traditional Chinese Medicine, Tianjin, People’s Republic of China, Tel +86 022 16622507882, Email doctor.wuyh@gmail.comAbstract: In our manuscript, we present a case study of siblings with Generalized Pustular Psoriasis (GPP) and Acrodermatitis Continua of Hallopeau (ACH), both harboring IL36RN gene mutations. The 3-year-old proband exhibited systemic pustules leading to a GPP diagnosis, while his 6-year-old sister developed nail ulcers and subungual pustules characteristic of ACH. Despite standard treatments, their conditions were refractory. Genetic analysis revealed a homozygous splice variant c.115+6 T>C, with heterozygous parents. This case underscores the role of IL36RN mutations in pustular psoriasis and supports ACH as a localized form of the disease. The distinct subtypes in siblings with identical mutations suggest a complex pathogenesis influenced by additional factors. Our findings highlight the importance of genetic testing in pustular psoriasis and warrant further investigation into the phenotypic variability of IL36RN-related disease.Keywords: Acrodermatitis Continua of Hallopeau, generalised pustular psoriasis, IL36RN gene mutationshttps://www.dovepress.com/acrodermatitis-continua-of-hallopeau-and-generalised-pustular-psoriasi-peer-reviewed-fulltext-article-PTTacrodermatitis continua of hallopeaugeneralised pustular psoriasisil36rn gene mutations
spellingShingle Gu M
Huang H
Xiao Z
Meng F
Sheng H
Lin Z
Li C
Wu Y
Acrodermatitis Continua of Hallopeau and Generalised Pustular Psoriasis: Case Reports of Two Different Manifestations of IL36RN Mutation in Siblings
Psoriasis: Targets and Therapy
acrodermatitis continua of hallopeau
generalised pustular psoriasis
il36rn gene mutations
title Acrodermatitis Continua of Hallopeau and Generalised Pustular Psoriasis: Case Reports of Two Different Manifestations of IL36RN Mutation in Siblings
title_full Acrodermatitis Continua of Hallopeau and Generalised Pustular Psoriasis: Case Reports of Two Different Manifestations of IL36RN Mutation in Siblings
title_fullStr Acrodermatitis Continua of Hallopeau and Generalised Pustular Psoriasis: Case Reports of Two Different Manifestations of IL36RN Mutation in Siblings
title_full_unstemmed Acrodermatitis Continua of Hallopeau and Generalised Pustular Psoriasis: Case Reports of Two Different Manifestations of IL36RN Mutation in Siblings
title_short Acrodermatitis Continua of Hallopeau and Generalised Pustular Psoriasis: Case Reports of Two Different Manifestations of IL36RN Mutation in Siblings
title_sort acrodermatitis continua of hallopeau and generalised pustular psoriasis case reports of two different manifestations of il36rn mutation in siblings
topic acrodermatitis continua of hallopeau
generalised pustular psoriasis
il36rn gene mutations
url https://www.dovepress.com/acrodermatitis-continua-of-hallopeau-and-generalised-pustular-psoriasi-peer-reviewed-fulltext-article-PTT
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