Proof of concept pilot study to assess the utility of magnetic resonance extra-cellular volume quantification to diagnose advanced liver disease in people with Cystic Fibrosis.

<h4>Background</h4>Current diagnostic tools are limited in their ability to diagnose cystic fibrosis liver disease (CFLD) as disease is often focal in nature. Magnetic resonance extracellular volume quantification (MRI ECV) in the liver may have diagnostic utility in CFLD as a more selec...

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Main Authors: Daniel H Tewkesbury, Jennifer A Scott, Rowland J Bright-Thomas, Sue Liong, Josephine Naish, Velauthan Rudralingam, Karen Piper Hanley, Andrew M Jones, Varinder S Athwal
Format: Article
Language:English
Published: Public Library of Science (PLoS) 2025-01-01
Series:PLoS ONE
Online Access:https://doi.org/10.1371/journal.pone.0318085
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author Daniel H Tewkesbury
Jennifer A Scott
Rowland J Bright-Thomas
Sue Liong
Josephine Naish
Velauthan Rudralingam
Karen Piper Hanley
Andrew M Jones
Varinder S Athwal
author_facet Daniel H Tewkesbury
Jennifer A Scott
Rowland J Bright-Thomas
Sue Liong
Josephine Naish
Velauthan Rudralingam
Karen Piper Hanley
Andrew M Jones
Varinder S Athwal
author_sort Daniel H Tewkesbury
collection DOAJ
description <h4>Background</h4>Current diagnostic tools are limited in their ability to diagnose cystic fibrosis liver disease (CFLD) as disease is often focal in nature. Magnetic resonance extracellular volume quantification (MRI ECV) in the liver may have diagnostic utility in CFLD as a more selective liver volume is assessed and can be performed using equipment readily available in clinical practice on a standard MRI protocol.<h4>Methods</h4>Healthy volunteers (HV), CF participants with no liver disease (CF-noLD) and CF participants with cirrhosis (CF-C) aged 18 years and above had MRI ECV measured using a 3T Siemens scanner. An additional retrospective analysis was performed to calculate MRI ECV in individuals who had available images obtained using a 1.5T Siemens scanner from a previous study.<h4>Results</h4>16 individuals had MRI ECV measured using a 3T Siemens scanner. Mean (SD) MRI ECV was 0.316 (0.058) for HV (n  =  5), 0.297 (0.034) for CF-noLD (n  =  5) and 0.388 (0.067) for CF-C (n  = 6 ). Post-hoc analysis showed a significant difference between CF-noLD and CF-C (p  =  0.046). Of 18 individuals with available images using a 1.5T scanner, mean (SD) MRI ECV was 0.269 (0.048) in HV (n  =  8), 0.310 (0.037) in CF-noLD (n  =  8) and 0.362 (0.063) in CF-C (n  =  2).<h4>Conclusions</h4>Liver MRI ECV quantification was feasible in adults with CF with no significant difference in results between 1.5T and 3T obtained images suggesting applicability across different types of MRI scanner. A higher MRI ECV was demonstrated in CF participants with cirrhosis suggesting potential utility as a diagnostic tool for those with advanced CFLD. Further evaluation in larger cohorts is warranted.
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spelling doaj-art-bf9f2cc988ae4961a6d6a9f9ef5b5c042025-08-20T03:52:47ZengPublic Library of Science (PLoS)PLoS ONE1932-62032025-01-01203e031808510.1371/journal.pone.0318085Proof of concept pilot study to assess the utility of magnetic resonance extra-cellular volume quantification to diagnose advanced liver disease in people with Cystic Fibrosis.Daniel H TewkesburyJennifer A ScottRowland J Bright-ThomasSue LiongJosephine NaishVelauthan RudralingamKaren Piper HanleyAndrew M JonesVarinder S Athwal<h4>Background</h4>Current diagnostic tools are limited in their ability to diagnose cystic fibrosis liver disease (CFLD) as disease is often focal in nature. Magnetic resonance extracellular volume quantification (MRI ECV) in the liver may have diagnostic utility in CFLD as a more selective liver volume is assessed and can be performed using equipment readily available in clinical practice on a standard MRI protocol.<h4>Methods</h4>Healthy volunteers (HV), CF participants with no liver disease (CF-noLD) and CF participants with cirrhosis (CF-C) aged 18 years and above had MRI ECV measured using a 3T Siemens scanner. An additional retrospective analysis was performed to calculate MRI ECV in individuals who had available images obtained using a 1.5T Siemens scanner from a previous study.<h4>Results</h4>16 individuals had MRI ECV measured using a 3T Siemens scanner. Mean (SD) MRI ECV was 0.316 (0.058) for HV (n  =  5), 0.297 (0.034) for CF-noLD (n  =  5) and 0.388 (0.067) for CF-C (n  = 6 ). Post-hoc analysis showed a significant difference between CF-noLD and CF-C (p  =  0.046). Of 18 individuals with available images using a 1.5T scanner, mean (SD) MRI ECV was 0.269 (0.048) in HV (n  =  8), 0.310 (0.037) in CF-noLD (n  =  8) and 0.362 (0.063) in CF-C (n  =  2).<h4>Conclusions</h4>Liver MRI ECV quantification was feasible in adults with CF with no significant difference in results between 1.5T and 3T obtained images suggesting applicability across different types of MRI scanner. A higher MRI ECV was demonstrated in CF participants with cirrhosis suggesting potential utility as a diagnostic tool for those with advanced CFLD. Further evaluation in larger cohorts is warranted.https://doi.org/10.1371/journal.pone.0318085
spellingShingle Daniel H Tewkesbury
Jennifer A Scott
Rowland J Bright-Thomas
Sue Liong
Josephine Naish
Velauthan Rudralingam
Karen Piper Hanley
Andrew M Jones
Varinder S Athwal
Proof of concept pilot study to assess the utility of magnetic resonance extra-cellular volume quantification to diagnose advanced liver disease in people with Cystic Fibrosis.
PLoS ONE
title Proof of concept pilot study to assess the utility of magnetic resonance extra-cellular volume quantification to diagnose advanced liver disease in people with Cystic Fibrosis.
title_full Proof of concept pilot study to assess the utility of magnetic resonance extra-cellular volume quantification to diagnose advanced liver disease in people with Cystic Fibrosis.
title_fullStr Proof of concept pilot study to assess the utility of magnetic resonance extra-cellular volume quantification to diagnose advanced liver disease in people with Cystic Fibrosis.
title_full_unstemmed Proof of concept pilot study to assess the utility of magnetic resonance extra-cellular volume quantification to diagnose advanced liver disease in people with Cystic Fibrosis.
title_short Proof of concept pilot study to assess the utility of magnetic resonance extra-cellular volume quantification to diagnose advanced liver disease in people with Cystic Fibrosis.
title_sort proof of concept pilot study to assess the utility of magnetic resonance extra cellular volume quantification to diagnose advanced liver disease in people with cystic fibrosis
url https://doi.org/10.1371/journal.pone.0318085
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