Multiomic analysis of human kidney disease identifies a tractable inflammatory and pro-fibrotic tubular cell phenotype

Abstract Maladaptive proximal tubular (PT) epithelial cells have been implicated in progression of chronic kidney disease (CKD), however the complexity of epithelial cell states within the fibrotic niche remains incompletely understood. Hence, we integrated snRNA and ATAC-seq with high-plex single-c...

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Main Authors: Maximilian Reck, David P. Baird, Stefan Veizades, Callum Sutherland, Rachel M. B. Bell, Heeyoun Hur, Carolynn Cairns, Piotr P. Janas, Ross Campbell, Andy Nam, Wei Yang, Nathan Schurman, Claire Williams, Eoin O’Sullivan, Meryam Beniazza, Andrea Corsinotti, Christopher Bellamy, Jeremy Hughes, Alexander Laird, Laura Denby, Tamir Chandra, David A. Ferenbach, Bryan R. Conway
Format: Article
Language:English
Published: Nature Portfolio 2025-05-01
Series:Nature Communications
Online Access:https://doi.org/10.1038/s41467-025-59997-4
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author Maximilian Reck
David P. Baird
Stefan Veizades
Callum Sutherland
Rachel M. B. Bell
Heeyoun Hur
Carolynn Cairns
Piotr P. Janas
Ross Campbell
Andy Nam
Wei Yang
Nathan Schurman
Claire Williams
Eoin O’Sullivan
Meryam Beniazza
Andrea Corsinotti
Christopher Bellamy
Jeremy Hughes
Alexander Laird
Laura Denby
Tamir Chandra
David A. Ferenbach
Bryan R. Conway
author_facet Maximilian Reck
David P. Baird
Stefan Veizades
Callum Sutherland
Rachel M. B. Bell
Heeyoun Hur
Carolynn Cairns
Piotr P. Janas
Ross Campbell
Andy Nam
Wei Yang
Nathan Schurman
Claire Williams
Eoin O’Sullivan
Meryam Beniazza
Andrea Corsinotti
Christopher Bellamy
Jeremy Hughes
Alexander Laird
Laura Denby
Tamir Chandra
David A. Ferenbach
Bryan R. Conway
author_sort Maximilian Reck
collection DOAJ
description Abstract Maladaptive proximal tubular (PT) epithelial cells have been implicated in progression of chronic kidney disease (CKD), however the complexity of epithelial cell states within the fibrotic niche remains incompletely understood. Hence, we integrated snRNA and ATAC-seq with high-plex single-cell molecular imaging to generate a spatially-revolved multiomic atlas of human kidney disease. We demonstrate that in injured kidneys, a subset of HAVCR1 + VCAM1 + PT cells acquired an inflammatory phenotype, upregulating genes encoding chemokines, pro-fibrotic and senescence-associated proteins and adhesion molecules including ICAM1. Spatial transcriptomic and multiplex-immunofluorescence determined that specifically these VCAM1+ICAM1+ inflammatory PT cells localised to the fibrotic niche. Ligand-receptor analysis highlighted paracrine signaling from inflammatory PT cells mediating leucocyte recruitment and myofibroblast activation. Loss of HNF4α and activation of NF-κβ and AP-1 transcription factors epigenetically imprinted the inflammatory phenotype. Targeting inflammatory tubular cells by administering an AP-1 inhibitor or senolytic agent ameliorated inflammation and fibrosis in murine models of kidney injury, hence these cells may be a tractable target in CKD.
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spelling doaj-art-b9a4b8406f164946a8482841d8dfc5042025-08-20T03:08:43ZengNature PortfolioNature Communications2041-17232025-05-0116112310.1038/s41467-025-59997-4Multiomic analysis of human kidney disease identifies a tractable inflammatory and pro-fibrotic tubular cell phenotypeMaximilian Reck0David P. Baird1Stefan Veizades2Callum Sutherland3Rachel M. B. Bell4Heeyoun Hur5Carolynn Cairns6Piotr P. Janas7Ross Campbell8Andy Nam9Wei Yang10Nathan Schurman11Claire Williams12Eoin O’Sullivan13Meryam Beniazza14Andrea Corsinotti15Christopher Bellamy16Jeremy Hughes17Alexander Laird18Laura Denby19Tamir Chandra20David A. Ferenbach21Bryan R. Conway22Centre for Cardiovascular Science, University of EdinburghCentre for Inflammation Research, University of EdinburghCentre for Cardiovascular Science, University of EdinburghCentre for Cardiovascular Science, University of EdinburghCentre for Cardiovascular Science, University of EdinburghCentre for Cardiovascular Science, University of EdinburghCentre for Cardiovascular Science, University of EdinburghCentre for Inflammation Research, University of EdinburghCentre for Inflammation Research, University of EdinburghBruker Spatial BiologyBruker Spatial BiologyBruker Spatial BiologyBruker Spatial BiologyInstitute of Molecular Bioscience, University of QueenslandInstitute for Regeneration and Repair, University of EdinburghInstitute for Regeneration and Repair, University of EdinburghCentre for Inflammation Research, University of EdinburghCentre for Inflammation Research, University of EdinburghInstitute of Genetics and Cancer, University of EdinburghCentre for Cardiovascular Science, University of EdinburghMRC Human Genetics Unit, University of EdinburghCentre for Inflammation Research, University of EdinburghCentre for Cardiovascular Science, University of EdinburghAbstract Maladaptive proximal tubular (PT) epithelial cells have been implicated in progression of chronic kidney disease (CKD), however the complexity of epithelial cell states within the fibrotic niche remains incompletely understood. Hence, we integrated snRNA and ATAC-seq with high-plex single-cell molecular imaging to generate a spatially-revolved multiomic atlas of human kidney disease. We demonstrate that in injured kidneys, a subset of HAVCR1 + VCAM1 + PT cells acquired an inflammatory phenotype, upregulating genes encoding chemokines, pro-fibrotic and senescence-associated proteins and adhesion molecules including ICAM1. Spatial transcriptomic and multiplex-immunofluorescence determined that specifically these VCAM1+ICAM1+ inflammatory PT cells localised to the fibrotic niche. Ligand-receptor analysis highlighted paracrine signaling from inflammatory PT cells mediating leucocyte recruitment and myofibroblast activation. Loss of HNF4α and activation of NF-κβ and AP-1 transcription factors epigenetically imprinted the inflammatory phenotype. Targeting inflammatory tubular cells by administering an AP-1 inhibitor or senolytic agent ameliorated inflammation and fibrosis in murine models of kidney injury, hence these cells may be a tractable target in CKD.https://doi.org/10.1038/s41467-025-59997-4
spellingShingle Maximilian Reck
David P. Baird
Stefan Veizades
Callum Sutherland
Rachel M. B. Bell
Heeyoun Hur
Carolynn Cairns
Piotr P. Janas
Ross Campbell
Andy Nam
Wei Yang
Nathan Schurman
Claire Williams
Eoin O’Sullivan
Meryam Beniazza
Andrea Corsinotti
Christopher Bellamy
Jeremy Hughes
Alexander Laird
Laura Denby
Tamir Chandra
David A. Ferenbach
Bryan R. Conway
Multiomic analysis of human kidney disease identifies a tractable inflammatory and pro-fibrotic tubular cell phenotype
Nature Communications
title Multiomic analysis of human kidney disease identifies a tractable inflammatory and pro-fibrotic tubular cell phenotype
title_full Multiomic analysis of human kidney disease identifies a tractable inflammatory and pro-fibrotic tubular cell phenotype
title_fullStr Multiomic analysis of human kidney disease identifies a tractable inflammatory and pro-fibrotic tubular cell phenotype
title_full_unstemmed Multiomic analysis of human kidney disease identifies a tractable inflammatory and pro-fibrotic tubular cell phenotype
title_short Multiomic analysis of human kidney disease identifies a tractable inflammatory and pro-fibrotic tubular cell phenotype
title_sort multiomic analysis of human kidney disease identifies a tractable inflammatory and pro fibrotic tubular cell phenotype
url https://doi.org/10.1038/s41467-025-59997-4
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