Prognostic factors for recurrence in acquired hemophilia A-results from a long-term observational study

Objectives: Acquired hemophilia A (AHA) is a rare autoimmune disease caused by autoantibodies against factor (F)VIII (FVIII), potentially leading to life-threatening bleeding. While predictors for remission have been analyzed, data on recurrence is lacking. Methods: This study investigated predictor...

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Main Authors: Lisa Reich, Florian Gatzke, Steffen Rauchfuss, Stefanie Roth, Wolfgang Miesbach
Format: Article
Language:English
Published: Elsevier 2025-02-01
Series:Research and Practice in Thrombosis and Haemostasis
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Online Access:http://www.sciencedirect.com/science/article/pii/S2475037925000317
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author Lisa Reich
Florian Gatzke
Steffen Rauchfuss
Stefanie Roth
Wolfgang Miesbach
author_facet Lisa Reich
Florian Gatzke
Steffen Rauchfuss
Stefanie Roth
Wolfgang Miesbach
author_sort Lisa Reich
collection DOAJ
description Objectives: Acquired hemophilia A (AHA) is a rare autoimmune disease caused by autoantibodies against factor (F)VIII (FVIII), potentially leading to life-threatening bleeding. While predictors for remission have been analyzed, data on recurrence is lacking. Methods: This study investigated predictors of AHA recurrence in 41 patients. Patients were divided into 2 groups: those with recurrence (n = 18) and those in stable long-term remission (n = 23) with at least 1 year of follow-up. Results: All relapses occurred within 1 year of initial remission. The median follow-up period was 3.8 years (IQR, 1.8-6.4) for all included patients. Multivariate Cox regression analysis revealed that initial FVIII activity <1 IU/dL and failure to achieve initial complete remission (CR) were significant predictors of relapse. Kaplan–Meier curves showed significantly different relapse-free survival rates for patients with initial FVIII activity <1 IU/dL vs ≥1 IU/dL (χ2[1] = 5.950, P = .015), and for those achieving initial CR vs partial remission (χ2[1] = 6.570, P = .010).Other factors such as inhibitor titer, gender, age, World Health Organization scale, underlying disorder, controlled disorder, initial immunosuppressive therapy, immunosuppressive therapy escalation, and partial remission at day 21 showed no significant relation to recurrences. Overall survival did not differ significantly between relapsing and nonrelapsing patients (χ2[1] = .896, P = .344). Conclusion: Initial FVIII <1 IU/dL and failure to achieve initial CR are identified as risk factors for recurrence in AHA. Patients with these characteristics should be closely monitored for at least 1 year after initial remission due to increased recurrence risk.
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spelling doaj-art-a80e3b84b73c4b81a886493fb72f6ba82025-08-20T02:18:23ZengElsevierResearch and Practice in Thrombosis and Haemostasis2475-03792025-02-019210270710.1016/j.rpth.2025.102707Prognostic factors for recurrence in acquired hemophilia A-results from a long-term observational studyLisa Reich0Florian Gatzke1Steffen Rauchfuss2Stefanie Roth3Wolfgang Miesbach4Medical Clinic 2, University Hospital Frankfurt, GermanyMedical Clinic 2, University Hospital Frankfurt, GermanyMedical Clinic 2, University Hospital Frankfurt, GermanyMedical Clinic 2, University Hospital Frankfurt, GermanyCorrespondence Wolfgang Miesbach, Medical Clinic 2, University Hospital Frankfurt, Theodor-Stern-Kai 7, 60590 Frankfurt, Germany.; Medical Clinic 2, University Hospital Frankfurt, GermanyObjectives: Acquired hemophilia A (AHA) is a rare autoimmune disease caused by autoantibodies against factor (F)VIII (FVIII), potentially leading to life-threatening bleeding. While predictors for remission have been analyzed, data on recurrence is lacking. Methods: This study investigated predictors of AHA recurrence in 41 patients. Patients were divided into 2 groups: those with recurrence (n = 18) and those in stable long-term remission (n = 23) with at least 1 year of follow-up. Results: All relapses occurred within 1 year of initial remission. The median follow-up period was 3.8 years (IQR, 1.8-6.4) for all included patients. Multivariate Cox regression analysis revealed that initial FVIII activity <1 IU/dL and failure to achieve initial complete remission (CR) were significant predictors of relapse. Kaplan–Meier curves showed significantly different relapse-free survival rates for patients with initial FVIII activity <1 IU/dL vs ≥1 IU/dL (χ2[1] = 5.950, P = .015), and for those achieving initial CR vs partial remission (χ2[1] = 6.570, P = .010).Other factors such as inhibitor titer, gender, age, World Health Organization scale, underlying disorder, controlled disorder, initial immunosuppressive therapy, immunosuppressive therapy escalation, and partial remission at day 21 showed no significant relation to recurrences. Overall survival did not differ significantly between relapsing and nonrelapsing patients (χ2[1] = .896, P = .344). Conclusion: Initial FVIII <1 IU/dL and failure to achieve initial CR are identified as risk factors for recurrence in AHA. Patients with these characteristics should be closely monitored for at least 1 year after initial remission due to increased recurrence risk.http://www.sciencedirect.com/science/article/pii/S2475037925000317acquired hemophiliableedingfactor VIIIrecurrenceremission
spellingShingle Lisa Reich
Florian Gatzke
Steffen Rauchfuss
Stefanie Roth
Wolfgang Miesbach
Prognostic factors for recurrence in acquired hemophilia A-results from a long-term observational study
Research and Practice in Thrombosis and Haemostasis
acquired hemophilia
bleeding
factor VIII
recurrence
remission
title Prognostic factors for recurrence in acquired hemophilia A-results from a long-term observational study
title_full Prognostic factors for recurrence in acquired hemophilia A-results from a long-term observational study
title_fullStr Prognostic factors for recurrence in acquired hemophilia A-results from a long-term observational study
title_full_unstemmed Prognostic factors for recurrence in acquired hemophilia A-results from a long-term observational study
title_short Prognostic factors for recurrence in acquired hemophilia A-results from a long-term observational study
title_sort prognostic factors for recurrence in acquired hemophilia a results from a long term observational study
topic acquired hemophilia
bleeding
factor VIII
recurrence
remission
url http://www.sciencedirect.com/science/article/pii/S2475037925000317
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AT floriangatzke prognosticfactorsforrecurrenceinacquiredhemophiliaaresultsfromalongtermobservationalstudy
AT steffenrauchfuss prognosticfactorsforrecurrenceinacquiredhemophiliaaresultsfromalongtermobservationalstudy
AT stefanieroth prognosticfactorsforrecurrenceinacquiredhemophiliaaresultsfromalongtermobservationalstudy
AT wolfgangmiesbach prognosticfactorsforrecurrenceinacquiredhemophiliaaresultsfromalongtermobservationalstudy