Adult Nesidioblastosis in Chronic Kidney Disease

Context. Nesidioblastosis is a rare cause of hyperinsulinemic hypoglycemia in adults. The diagnosis is further complicated in patients with kidney failure, since impaired renal function can cause hypoglycemia by itself and diagnostic criteria for this clinical scenario have not been developed yet. C...

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Main Authors: Eduardo Lozano-Melendez, Mercedes Aguilar-Soto, Luis Eugenio Graniel-Palafox, Laura Elena Ceceña-Martínez, Rafael Valdez-Ortiz, Fabio Solis-Jimenez
Format: Article
Language:English
Published: Wiley 2019-01-01
Series:Case Reports in Endocrinology
Online Access:http://dx.doi.org/10.1155/2019/7640384
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author Eduardo Lozano-Melendez
Mercedes Aguilar-Soto
Luis Eugenio Graniel-Palafox
Laura Elena Ceceña-Martínez
Rafael Valdez-Ortiz
Fabio Solis-Jimenez
author_facet Eduardo Lozano-Melendez
Mercedes Aguilar-Soto
Luis Eugenio Graniel-Palafox
Laura Elena Ceceña-Martínez
Rafael Valdez-Ortiz
Fabio Solis-Jimenez
author_sort Eduardo Lozano-Melendez
collection DOAJ
description Context. Nesidioblastosis is a rare cause of hyperinsulinemic hypoglycemia in adults. The diagnosis is further complicated in patients with kidney failure, since impaired renal function can cause hypoglycemia by itself and diagnostic criteria for this clinical scenario have not been developed yet. Case Description. We present the case report of a 36-year-old patient with end stage chronic kidney disease who presented to the emergency department because of hypoglycemia. However, the patient’s hypoglycemia did not respond well to medical treatment; the diagnosis of hyperinsulinemic hypoglycemia was made due to the presence of inappropriately high levels of insulin, proinsulin, and C-peptide during an episode of hypoglycemia. Imaging studies were performed without any conclusive findings; so selective intra-arterial pancreatic stimulation with hepatic venous sampling (SACTS) was done. Based on the results of this study the patient was referred for subtotal pancreatectomy. Classic criteria for the diagnosis of insulinoma with SACTS required a 2-fold increase in insulin levels but newer criteria suggest thresholds that are useful in the differential diagnosis of insulinoma and nesidioblastosis. In our patient, the former criteria were positive; however, the new criteria were not compatible with insulinoma but with nesidioblastosis, which was the final histopathological diagnosis. Conclusion. This seems to be the first case report of a patient with end stage chronic kidney disease and nesidioblastosis, as well as the first case of hyperinsulinemic hypoglycemia in the context of kidney failure diagnosed by SACTS. We consider this method to be very useful in patients with renal impairment because peripancreatic insulin levels do not depend on the renal function.
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spelling doaj-art-9b51ce0b52df487b9e74c5b370711dc72025-08-20T02:20:26ZengWileyCase Reports in Endocrinology2090-65012090-651X2019-01-01201910.1155/2019/76403847640384Adult Nesidioblastosis in Chronic Kidney DiseaseEduardo Lozano-Melendez0Mercedes Aguilar-Soto1Luis Eugenio Graniel-Palafox2Laura Elena Ceceña-Martínez3Rafael Valdez-Ortiz4Fabio Solis-Jimenez5Faculty of Medicine and Nutrition of the Juarez University of the State of Durango, Durango, Durango, MexicoDepartment of Internal Medicine, ABC Medical Center, Mexico City, MexicoDepartment of Vascular and Interventional Radiology, General Hospital of Mexico ‘Dr. Eduardo Liceaga’, Mexico City, MexicoDepartment of Internal, General Hospital of Mexico ‘Dr. Eduardo Liceaga’, Mexico City, MexicoDepartment of Nephrology, General Hospital of Mexico ‘Dr. Eduardo Liceaga’, Mexico City, MexicoDepartment of Internal, General Hospital of Mexico ‘Dr. Eduardo Liceaga’, Mexico City, MexicoContext. Nesidioblastosis is a rare cause of hyperinsulinemic hypoglycemia in adults. The diagnosis is further complicated in patients with kidney failure, since impaired renal function can cause hypoglycemia by itself and diagnostic criteria for this clinical scenario have not been developed yet. Case Description. We present the case report of a 36-year-old patient with end stage chronic kidney disease who presented to the emergency department because of hypoglycemia. However, the patient’s hypoglycemia did not respond well to medical treatment; the diagnosis of hyperinsulinemic hypoglycemia was made due to the presence of inappropriately high levels of insulin, proinsulin, and C-peptide during an episode of hypoglycemia. Imaging studies were performed without any conclusive findings; so selective intra-arterial pancreatic stimulation with hepatic venous sampling (SACTS) was done. Based on the results of this study the patient was referred for subtotal pancreatectomy. Classic criteria for the diagnosis of insulinoma with SACTS required a 2-fold increase in insulin levels but newer criteria suggest thresholds that are useful in the differential diagnosis of insulinoma and nesidioblastosis. In our patient, the former criteria were positive; however, the new criteria were not compatible with insulinoma but with nesidioblastosis, which was the final histopathological diagnosis. Conclusion. This seems to be the first case report of a patient with end stage chronic kidney disease and nesidioblastosis, as well as the first case of hyperinsulinemic hypoglycemia in the context of kidney failure diagnosed by SACTS. We consider this method to be very useful in patients with renal impairment because peripancreatic insulin levels do not depend on the renal function.http://dx.doi.org/10.1155/2019/7640384
spellingShingle Eduardo Lozano-Melendez
Mercedes Aguilar-Soto
Luis Eugenio Graniel-Palafox
Laura Elena Ceceña-Martínez
Rafael Valdez-Ortiz
Fabio Solis-Jimenez
Adult Nesidioblastosis in Chronic Kidney Disease
Case Reports in Endocrinology
title Adult Nesidioblastosis in Chronic Kidney Disease
title_full Adult Nesidioblastosis in Chronic Kidney Disease
title_fullStr Adult Nesidioblastosis in Chronic Kidney Disease
title_full_unstemmed Adult Nesidioblastosis in Chronic Kidney Disease
title_short Adult Nesidioblastosis in Chronic Kidney Disease
title_sort adult nesidioblastosis in chronic kidney disease
url http://dx.doi.org/10.1155/2019/7640384
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