Anti-angiogenic tyrosine kinase inhibitors and the pathophysiology of their toxic effects: revisiting the treatment of anemia in metastatic cancers

Abstract Background Anti-angiogenic tyrosine kinase inhibitors (TKIs) have become major drugs for the treatment of various cancer types, but with an overall high incidence of severe toxicities, particularly haematological toxicities including severe anemia. Methods We treated C57BL6 mice continuousl...

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Main Authors: Tai Van Nguyen, Eurydice Angeli, Diaddin Hamdan, Morad El Bouchtaoui, Oanh T. Bui, Feriel Azibani, Rong Shen, He Lu, Kien Hung Do, Anne Janin, Quang Van Le, Guilhem Bousquet
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Language:English
Published: BMC 2025-04-01
Series:Experimental Hematology & Oncology
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Online Access:https://doi.org/10.1186/s40164-025-00640-9
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author Tai Van Nguyen
Eurydice Angeli
Diaddin Hamdan
Morad El Bouchtaoui
Oanh T. Bui
Feriel Azibani
Rong Shen
He Lu
Kien Hung Do
Anne Janin
Quang Van Le
Guilhem Bousquet
author_facet Tai Van Nguyen
Eurydice Angeli
Diaddin Hamdan
Morad El Bouchtaoui
Oanh T. Bui
Feriel Azibani
Rong Shen
He Lu
Kien Hung Do
Anne Janin
Quang Van Le
Guilhem Bousquet
author_sort Tai Van Nguyen
collection DOAJ
description Abstract Background Anti-angiogenic tyrosine kinase inhibitors (TKIs) have become major drugs for the treatment of various cancer types, but with an overall high incidence of severe toxicities, particularly haematological toxicities including severe anemia. Methods We treated C57BL6 mice continuously by gavage for 14 days with either sunitinib, pazopanib, or axitinib. In this study, we set out to decipher the pathophysiological mechanisms of anti-angiogenic TKI haematological toxicity. Results We demonstrated that anti-angiogenic TKIs induced a broad range of toxic effects on normal tissues through a cytotoxic effect on normal endothelial cells. Haematological toxicities were particulary marked with sunitinib. Sunitinib-induced hypoxia through the destruction of normal vessels in the bone marrow mainly affected erythrocyte and myeloid lineages, and this was associated with a blockage in erythrocyte maturation. Althought sunitinib-induced anemia was associated with an adaptative response to systemic hypoxia, we demonstrated that erythropoietin (EPO) concentrations in the total bone marrow of sunitinib-treated mice were significantly lower than in untreated mice. This is coherent with the destruction of microvessels in the bone marrow under sunitinib treatment, preventing circulating EPO from reaching the bone marrow at relevant concentrations. However, we demonstrated an additional effect specific to sunitinib that induced autophagy flux inhibition in erythroid progenitors, with a blockage of erythrocyte maturation, leading to more severe anemia. Conclusions We deciphered the pathophysiology of anti-angiogenic TKI-induced anemia, which we observed to be mainly linked to a direct effect on normal bone-marrow vessels and to autophagy flux inhibition in erythroid progenitors under sunitinib.
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spelling doaj-art-92bc65bdcfea49ffb13e49e3a5fd1df72025-08-20T02:17:49ZengBMCExperimental Hematology & Oncology2162-36192025-04-011411610.1186/s40164-025-00640-9Anti-angiogenic tyrosine kinase inhibitors and the pathophysiology of their toxic effects: revisiting the treatment of anemia in metastatic cancersTai Van Nguyen0Eurydice Angeli1Diaddin Hamdan2Morad El Bouchtaoui3Oanh T. Bui4Feriel Azibani5Rong Shen6He Lu7Kien Hung Do8Anne Janin9Quang Van Le10Guilhem Bousquet11Université de Paris, INSERM, MASCOTUniversité de Paris, INSERM, MASCOTUniversité de Paris, INSERM, MASCOTUniversité de Paris, INSERM, MASCOTUniversité de Paris, INSERM, MASCOTUniversité de Paris, INSERM, MASCOTDepartment of Hematology, Shanghai Institute of Hematology, Ruijin Hospital Affiliated to Shanghai Jiao Tong University School of MedicineUniversité de Paris, INSERM, MASCOTVietnam National Cancer Hospital – K HospitalUniversité de Paris, INSERM, MASCOTVietnam National Cancer Hospital – K HospitalUniversité de Paris, INSERM, MASCOTAbstract Background Anti-angiogenic tyrosine kinase inhibitors (TKIs) have become major drugs for the treatment of various cancer types, but with an overall high incidence of severe toxicities, particularly haematological toxicities including severe anemia. Methods We treated C57BL6 mice continuously by gavage for 14 days with either sunitinib, pazopanib, or axitinib. In this study, we set out to decipher the pathophysiological mechanisms of anti-angiogenic TKI haematological toxicity. Results We demonstrated that anti-angiogenic TKIs induced a broad range of toxic effects on normal tissues through a cytotoxic effect on normal endothelial cells. Haematological toxicities were particulary marked with sunitinib. Sunitinib-induced hypoxia through the destruction of normal vessels in the bone marrow mainly affected erythrocyte and myeloid lineages, and this was associated with a blockage in erythrocyte maturation. Althought sunitinib-induced anemia was associated with an adaptative response to systemic hypoxia, we demonstrated that erythropoietin (EPO) concentrations in the total bone marrow of sunitinib-treated mice were significantly lower than in untreated mice. This is coherent with the destruction of microvessels in the bone marrow under sunitinib treatment, preventing circulating EPO from reaching the bone marrow at relevant concentrations. However, we demonstrated an additional effect specific to sunitinib that induced autophagy flux inhibition in erythroid progenitors, with a blockage of erythrocyte maturation, leading to more severe anemia. Conclusions We deciphered the pathophysiology of anti-angiogenic TKI-induced anemia, which we observed to be mainly linked to a direct effect on normal bone-marrow vessels and to autophagy flux inhibition in erythroid progenitors under sunitinib.https://doi.org/10.1186/s40164-025-00640-9Anti-angiogenic agentsTyrosine kinase inhibitorAnemiaSunitinibAutophagyErythropoietin
spellingShingle Tai Van Nguyen
Eurydice Angeli
Diaddin Hamdan
Morad El Bouchtaoui
Oanh T. Bui
Feriel Azibani
Rong Shen
He Lu
Kien Hung Do
Anne Janin
Quang Van Le
Guilhem Bousquet
Anti-angiogenic tyrosine kinase inhibitors and the pathophysiology of their toxic effects: revisiting the treatment of anemia in metastatic cancers
Experimental Hematology & Oncology
Anti-angiogenic agents
Tyrosine kinase inhibitor
Anemia
Sunitinib
Autophagy
Erythropoietin
title Anti-angiogenic tyrosine kinase inhibitors and the pathophysiology of their toxic effects: revisiting the treatment of anemia in metastatic cancers
title_full Anti-angiogenic tyrosine kinase inhibitors and the pathophysiology of their toxic effects: revisiting the treatment of anemia in metastatic cancers
title_fullStr Anti-angiogenic tyrosine kinase inhibitors and the pathophysiology of their toxic effects: revisiting the treatment of anemia in metastatic cancers
title_full_unstemmed Anti-angiogenic tyrosine kinase inhibitors and the pathophysiology of their toxic effects: revisiting the treatment of anemia in metastatic cancers
title_short Anti-angiogenic tyrosine kinase inhibitors and the pathophysiology of their toxic effects: revisiting the treatment of anemia in metastatic cancers
title_sort anti angiogenic tyrosine kinase inhibitors and the pathophysiology of their toxic effects revisiting the treatment of anemia in metastatic cancers
topic Anti-angiogenic agents
Tyrosine kinase inhibitor
Anemia
Sunitinib
Autophagy
Erythropoietin
url https://doi.org/10.1186/s40164-025-00640-9
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