Visceral Myopathy Presenting as Acute Appendicitis and Ogilvie Syndrome

Background. Visceral myopathy is rare pathological condition of gastrointestinal tract with uncertain clinical presentation and unknown etiology. It often presents with symptoms of chronic intestinal pseudoobstruction of colon. We report a case of visceral myopathy which presented to us as acute ap...

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Main Authors: Punyaram Kharbuja, Raghvendra Thakur, Jian Suo
Format: Article
Language:English
Published: Wiley 2013-01-01
Series:Case Reports in Surgery
Online Access:http://dx.doi.org/10.1155/2013/906457
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author Punyaram Kharbuja
Raghvendra Thakur
Jian Suo
author_facet Punyaram Kharbuja
Raghvendra Thakur
Jian Suo
author_sort Punyaram Kharbuja
collection DOAJ
description Background. Visceral myopathy is rare pathological condition of gastrointestinal tract with uncertain clinical presentation and unknown etiology. It often presents with symptoms of chronic intestinal pseudoobstruction of colon. We report a case of visceral myopathy which presented to us as acute appendicitis and Ogilvie syndrome, and we managed it surgically. Method and Result. A case report of 20-year female clinically presented as acute appendicitis and we performed laparoscopic exploration which revealed inflamed appendix with grossly dilated ascending colon. We performed laparoscopic appendectomy and postoperatively managed the patients with IV fluids, antibiotics, neostigmine, and extended length rectal tube for enema and decompression. During postoperative period, she developed abdomen distension and peritonitis, and we ordered abdomen CT which revealed colon pseudo- obstruction. We performed right hemicolectomy with permanent ileostomy, and the histopathology reports of resected colon were visceral myopathy. Conclusion. Visceral myopathy is very rare group of disease and poorly understood condition that may present with chronic or acute intestinal pseudo-obstruction and often mimic other more common gastrointestinal disease. VM should be considered as differential diagnosis whenever the patient presents with acute appendicitis, uncharacteristic abdominal symptoms, recurrent attacks of abdominal distention, and pain with no radiological evidence of intestinal obstruction.
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spelling doaj-art-7aa2338588a84f8ba19989e0a11f25592025-02-03T01:12:34ZengWileyCase Reports in Surgery2090-69002090-69192013-01-01201310.1155/2013/906457906457Visceral Myopathy Presenting as Acute Appendicitis and Ogilvie SyndromePunyaram Kharbuja0Raghvendra Thakur1Jian Suo2Department of Gastrointestinal-Colorectal Surgery, First Hospital of Jilin University, 71th Xin Min Street, Changchun, Jilin 130021, ChinaDepartment of Gastrointestinal-Colorectal Surgery, First Hospital of Jilin University, 71th Xin Min Street, Changchun, Jilin 130021, ChinaDepartment of Gastrointestinal-Colorectal Surgery, First Hospital of Jilin University, 71th Xin Min Street, Changchun, Jilin 130021, ChinaBackground. Visceral myopathy is rare pathological condition of gastrointestinal tract with uncertain clinical presentation and unknown etiology. It often presents with symptoms of chronic intestinal pseudoobstruction of colon. We report a case of visceral myopathy which presented to us as acute appendicitis and Ogilvie syndrome, and we managed it surgically. Method and Result. A case report of 20-year female clinically presented as acute appendicitis and we performed laparoscopic exploration which revealed inflamed appendix with grossly dilated ascending colon. We performed laparoscopic appendectomy and postoperatively managed the patients with IV fluids, antibiotics, neostigmine, and extended length rectal tube for enema and decompression. During postoperative period, she developed abdomen distension and peritonitis, and we ordered abdomen CT which revealed colon pseudo- obstruction. We performed right hemicolectomy with permanent ileostomy, and the histopathology reports of resected colon were visceral myopathy. Conclusion. Visceral myopathy is very rare group of disease and poorly understood condition that may present with chronic or acute intestinal pseudo-obstruction and often mimic other more common gastrointestinal disease. VM should be considered as differential diagnosis whenever the patient presents with acute appendicitis, uncharacteristic abdominal symptoms, recurrent attacks of abdominal distention, and pain with no radiological evidence of intestinal obstruction.http://dx.doi.org/10.1155/2013/906457
spellingShingle Punyaram Kharbuja
Raghvendra Thakur
Jian Suo
Visceral Myopathy Presenting as Acute Appendicitis and Ogilvie Syndrome
Case Reports in Surgery
title Visceral Myopathy Presenting as Acute Appendicitis and Ogilvie Syndrome
title_full Visceral Myopathy Presenting as Acute Appendicitis and Ogilvie Syndrome
title_fullStr Visceral Myopathy Presenting as Acute Appendicitis and Ogilvie Syndrome
title_full_unstemmed Visceral Myopathy Presenting as Acute Appendicitis and Ogilvie Syndrome
title_short Visceral Myopathy Presenting as Acute Appendicitis and Ogilvie Syndrome
title_sort visceral myopathy presenting as acute appendicitis and ogilvie syndrome
url http://dx.doi.org/10.1155/2013/906457
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