Mandibular Osteitis Leading to the Diagnosis of SAPHO Syndrome
Synovitis, acne, pustulosis, hyperostosis, and osteitis (SAPHO) syndrome is a disorder characterized by pustular skin lesions and osteoarticular lesions. Mandibular involvement of SAPHO syndrome is clinically rare, and it is difficult to reach a diagnosis of SAPHO syndrome from only mandibular manif...
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| Main Authors: | , , , , |
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| Format: | Article |
| Language: | English |
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Wiley
2018-01-01
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| Series: | Case Reports in Radiology |
| Online Access: | http://dx.doi.org/10.1155/2018/9142362 |
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| author | Tomohiro Kikuchi Hiroyuki Fujii Akifumi Fujita Tomoko Sugiyama Hideharu Sugimoto |
| author_facet | Tomohiro Kikuchi Hiroyuki Fujii Akifumi Fujita Tomoko Sugiyama Hideharu Sugimoto |
| author_sort | Tomohiro Kikuchi |
| collection | DOAJ |
| description | Synovitis, acne, pustulosis, hyperostosis, and osteitis (SAPHO) syndrome is a disorder characterized by pustular skin lesions and osteoarticular lesions. Mandibular involvement of SAPHO syndrome is clinically rare, and it is difficult to reach a diagnosis of SAPHO syndrome from only mandibular manifestations. This report describes the case of a 26-year-old woman who presented with mandibular osteitis. Orthopantomogram and computed tomography showed sclerotic change of the right body of the mandible with periosteal reaction without odontogenic infection, which suggested the possibility of SAPHO syndrome. Detailed medical interview found that she had a history of palmoplantar pustulosis treated at a local dermatology clinic and additional bone scintigraphy showed diffuse increased uptake in the right mandible, as well as in the sternum and the sternocostoclavicular joints. She was eventually diagnosed as having SAPHO syndrome. We should consider SAPHO syndrome when we encounter a patient with mandibular osteitis of unknown etiology. |
| format | Article |
| id | doaj-art-69c49c3f47e9468eb1c4ff383429e170 |
| institution | Kabale University |
| issn | 2090-6862 2090-6870 |
| language | English |
| publishDate | 2018-01-01 |
| publisher | Wiley |
| record_format | Article |
| series | Case Reports in Radiology |
| spelling | doaj-art-69c49c3f47e9468eb1c4ff383429e1702025-02-03T01:33:27ZengWileyCase Reports in Radiology2090-68622090-68702018-01-01201810.1155/2018/91423629142362Mandibular Osteitis Leading to the Diagnosis of SAPHO SyndromeTomohiro Kikuchi0Hiroyuki Fujii1Akifumi Fujita2Tomoko Sugiyama3Hideharu Sugimoto4Department of Radiology, Jichi Medical University, School of Medicine, 3311-1 Yakushiji, Shimotsuke, Tochigi 329-0498, JapanDepartment of Radiology, Jichi Medical University, School of Medicine, 3311-1 Yakushiji, Shimotsuke, Tochigi 329-0498, JapanDepartment of Radiology, Jichi Medical University, School of Medicine, 3311-1 Yakushiji, Shimotsuke, Tochigi 329-0498, JapanDepartment of Dentistry, Oral and Maxillofacial Surgery, Jichi Medical University, School of Medicine, 3311-1 Yakushiji, Shimotsuke, Tochigi 329-0498, JapanDepartment of Radiology, Jichi Medical University, School of Medicine, 3311-1 Yakushiji, Shimotsuke, Tochigi 329-0498, JapanSynovitis, acne, pustulosis, hyperostosis, and osteitis (SAPHO) syndrome is a disorder characterized by pustular skin lesions and osteoarticular lesions. Mandibular involvement of SAPHO syndrome is clinically rare, and it is difficult to reach a diagnosis of SAPHO syndrome from only mandibular manifestations. This report describes the case of a 26-year-old woman who presented with mandibular osteitis. Orthopantomogram and computed tomography showed sclerotic change of the right body of the mandible with periosteal reaction without odontogenic infection, which suggested the possibility of SAPHO syndrome. Detailed medical interview found that she had a history of palmoplantar pustulosis treated at a local dermatology clinic and additional bone scintigraphy showed diffuse increased uptake in the right mandible, as well as in the sternum and the sternocostoclavicular joints. She was eventually diagnosed as having SAPHO syndrome. We should consider SAPHO syndrome when we encounter a patient with mandibular osteitis of unknown etiology.http://dx.doi.org/10.1155/2018/9142362 |
| spellingShingle | Tomohiro Kikuchi Hiroyuki Fujii Akifumi Fujita Tomoko Sugiyama Hideharu Sugimoto Mandibular Osteitis Leading to the Diagnosis of SAPHO Syndrome Case Reports in Radiology |
| title | Mandibular Osteitis Leading to the Diagnosis of SAPHO Syndrome |
| title_full | Mandibular Osteitis Leading to the Diagnosis of SAPHO Syndrome |
| title_fullStr | Mandibular Osteitis Leading to the Diagnosis of SAPHO Syndrome |
| title_full_unstemmed | Mandibular Osteitis Leading to the Diagnosis of SAPHO Syndrome |
| title_short | Mandibular Osteitis Leading to the Diagnosis of SAPHO Syndrome |
| title_sort | mandibular osteitis leading to the diagnosis of sapho syndrome |
| url | http://dx.doi.org/10.1155/2018/9142362 |
| work_keys_str_mv | AT tomohirokikuchi mandibularosteitisleadingtothediagnosisofsaphosyndrome AT hiroyukifujii mandibularosteitisleadingtothediagnosisofsaphosyndrome AT akifumifujita mandibularosteitisleadingtothediagnosisofsaphosyndrome AT tomokosugiyama mandibularosteitisleadingtothediagnosisofsaphosyndrome AT hideharusugimoto mandibularosteitisleadingtothediagnosisofsaphosyndrome |