Identification of a sudden cardiac death susceptibility locus at 2q24.2 through genome-wide association in European ancestry individuals.

Sudden cardiac death (SCD) continues to be one of the leading causes of mortality worldwide, with an annual incidence estimated at 250,000-300,000 in the United States and with the vast majority occurring in the setting of coronary disease. We performed a genome-wide association meta-analysis in 1,2...

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Main Authors: Dan E Arking, M Juhani Junttila, Philippe Goyette, Adriana Huertas-Vazquez, Mark Eijgelsheim, Marieke T Blom, Christopher Newton-Cheh, Kyndaron Reinier, Carmen Teodorescu, Audrey Uy-Evanado, Naima Carter-Monroe, Kari S Kaikkonen, Marja-Leena Kortelainen, Gabrielle Boucher, Caroline Lagacé, Anna Moes, XiaoQing Zhao, Frank Kolodgie, Fernando Rivadeneira, Albert Hofman, Jacqueline C M Witteman, André G Uitterlinden, Roos F Marsman, Raha Pazoki, Abdennasser Bardai, Rudolph W Koster, Abbas Dehghan, Shih-Jen Hwang, Pallav Bhatnagar, Wendy Post, Gina Hilton, Ronald J Prineas, Man Li, Anna Köttgen, Georg Ehret, Eric Boerwinkle, Josef Coresh, W H Linda Kao, Bruce M Psaty, Gordon F Tomaselli, Nona Sotoodehnia, David S Siscovick, Greg L Burke, Eduardo Marbán, Peter M Spooner, L Adrienne Cupples, Jonathan Jui, Karen Gunson, Y Antero Kesäniemi, Arthur A M Wilde, Jean-Claude Tardif, Christopher J O'Donnell, Connie R Bezzina, Renu Virmani, Bruno H C H Stricker, Hanno L Tan, Christine M Albert, Aravinda Chakravarti, John D Rioux, Heikki V Huikuri, Sumeet S Chugh
Format: Article
Language:English
Published: Public Library of Science (PLoS) 2011-06-01
Series:PLoS Genetics
Online Access:https://journals.plos.org/plosgenetics/article/file?id=10.1371/journal.pgen.1002158&type=printable
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author Dan E Arking
M Juhani Junttila
Philippe Goyette
Adriana Huertas-Vazquez
Mark Eijgelsheim
Marieke T Blom
Christopher Newton-Cheh
Kyndaron Reinier
Carmen Teodorescu
Audrey Uy-Evanado
Naima Carter-Monroe
Kari S Kaikkonen
Marja-Leena Kortelainen
Gabrielle Boucher
Caroline Lagacé
Anna Moes
XiaoQing Zhao
Frank Kolodgie
Fernando Rivadeneira
Albert Hofman
Jacqueline C M Witteman
André G Uitterlinden
Roos F Marsman
Raha Pazoki
Abdennasser Bardai
Rudolph W Koster
Abbas Dehghan
Shih-Jen Hwang
Pallav Bhatnagar
Wendy Post
Gina Hilton
Ronald J Prineas
Man Li
Anna Köttgen
Georg Ehret
Eric Boerwinkle
Josef Coresh
W H Linda Kao
Bruce M Psaty
Gordon F Tomaselli
Nona Sotoodehnia
David S Siscovick
Greg L Burke
Eduardo Marbán
Peter M Spooner
L Adrienne Cupples
Jonathan Jui
Karen Gunson
Y Antero Kesäniemi
Arthur A M Wilde
Jean-Claude Tardif
Christopher J O'Donnell
Connie R Bezzina
Renu Virmani
Bruno H C H Stricker
Hanno L Tan
Christine M Albert
Aravinda Chakravarti
John D Rioux
Heikki V Huikuri
Sumeet S Chugh
author_facet Dan E Arking
M Juhani Junttila
Philippe Goyette
Adriana Huertas-Vazquez
Mark Eijgelsheim
Marieke T Blom
Christopher Newton-Cheh
Kyndaron Reinier
Carmen Teodorescu
Audrey Uy-Evanado
Naima Carter-Monroe
Kari S Kaikkonen
Marja-Leena Kortelainen
Gabrielle Boucher
Caroline Lagacé
Anna Moes
XiaoQing Zhao
Frank Kolodgie
Fernando Rivadeneira
Albert Hofman
Jacqueline C M Witteman
André G Uitterlinden
Roos F Marsman
Raha Pazoki
Abdennasser Bardai
Rudolph W Koster
Abbas Dehghan
Shih-Jen Hwang
Pallav Bhatnagar
Wendy Post
Gina Hilton
Ronald J Prineas
Man Li
Anna Köttgen
Georg Ehret
Eric Boerwinkle
Josef Coresh
W H Linda Kao
Bruce M Psaty
Gordon F Tomaselli
Nona Sotoodehnia
David S Siscovick
Greg L Burke
Eduardo Marbán
Peter M Spooner
L Adrienne Cupples
Jonathan Jui
Karen Gunson
Y Antero Kesäniemi
Arthur A M Wilde
Jean-Claude Tardif
Christopher J O'Donnell
Connie R Bezzina
Renu Virmani
Bruno H C H Stricker
Hanno L Tan
Christine M Albert
Aravinda Chakravarti
John D Rioux
Heikki V Huikuri
Sumeet S Chugh
author_sort Dan E Arking
collection DOAJ
description Sudden cardiac death (SCD) continues to be one of the leading causes of mortality worldwide, with an annual incidence estimated at 250,000-300,000 in the United States and with the vast majority occurring in the setting of coronary disease. We performed a genome-wide association meta-analysis in 1,283 SCD cases and >20,000 control individuals of European ancestry from 5 studies, with follow-up genotyping in up to 3,119 SCD cases and 11,146 controls from 11 European ancestry studies, and identify the BAZ2B locus as associated with SCD (P = 1.8×10(-10)). The risk allele, while ancestral, has a frequency of ~1.4%, suggesting strong negative selection and increases risk for SCD by 1.92-fold per allele (95% CI 1.57-2.34). We also tested the role of 49 SNPs previously implicated in modulating electrocardiographic traits (QRS, QT, and RR intervals). Consistent with epidemiological studies showing increased risk of SCD with prolonged QRS/QT intervals, the interval-prolonging alleles are in aggregate associated with increased risk for SCD (P = 0.006).
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spelling doaj-art-66b3fe689b1d46a3b42f17472cd2611c2025-08-20T02:30:55ZengPublic Library of Science (PLoS)PLoS Genetics1553-73901553-74042011-06-0176e100215810.1371/journal.pgen.1002158Identification of a sudden cardiac death susceptibility locus at 2q24.2 through genome-wide association in European ancestry individuals.Dan E ArkingM Juhani JunttilaPhilippe GoyetteAdriana Huertas-VazquezMark EijgelsheimMarieke T BlomChristopher Newton-ChehKyndaron ReinierCarmen TeodorescuAudrey Uy-EvanadoNaima Carter-MonroeKari S KaikkonenMarja-Leena KortelainenGabrielle BoucherCaroline LagacéAnna MoesXiaoQing ZhaoFrank KolodgieFernando RivadeneiraAlbert HofmanJacqueline C M WittemanAndré G UitterlindenRoos F MarsmanRaha PazokiAbdennasser BardaiRudolph W KosterAbbas DehghanShih-Jen HwangPallav BhatnagarWendy PostGina HiltonRonald J PrineasMan LiAnna KöttgenGeorg EhretEric BoerwinkleJosef CoreshW H Linda KaoBruce M PsatyGordon F TomaselliNona SotoodehniaDavid S SiscovickGreg L BurkeEduardo MarbánPeter M SpoonerL Adrienne CupplesJonathan JuiKaren GunsonY Antero KesäniemiArthur A M WildeJean-Claude TardifChristopher J O'DonnellConnie R BezzinaRenu VirmaniBruno H C H StrickerHanno L TanChristine M AlbertAravinda ChakravartiJohn D RiouxHeikki V HuikuriSumeet S ChughSudden cardiac death (SCD) continues to be one of the leading causes of mortality worldwide, with an annual incidence estimated at 250,000-300,000 in the United States and with the vast majority occurring in the setting of coronary disease. We performed a genome-wide association meta-analysis in 1,283 SCD cases and >20,000 control individuals of European ancestry from 5 studies, with follow-up genotyping in up to 3,119 SCD cases and 11,146 controls from 11 European ancestry studies, and identify the BAZ2B locus as associated with SCD (P = 1.8×10(-10)). The risk allele, while ancestral, has a frequency of ~1.4%, suggesting strong negative selection and increases risk for SCD by 1.92-fold per allele (95% CI 1.57-2.34). We also tested the role of 49 SNPs previously implicated in modulating electrocardiographic traits (QRS, QT, and RR intervals). Consistent with epidemiological studies showing increased risk of SCD with prolonged QRS/QT intervals, the interval-prolonging alleles are in aggregate associated with increased risk for SCD (P = 0.006).https://journals.plos.org/plosgenetics/article/file?id=10.1371/journal.pgen.1002158&type=printable
spellingShingle Dan E Arking
M Juhani Junttila
Philippe Goyette
Adriana Huertas-Vazquez
Mark Eijgelsheim
Marieke T Blom
Christopher Newton-Cheh
Kyndaron Reinier
Carmen Teodorescu
Audrey Uy-Evanado
Naima Carter-Monroe
Kari S Kaikkonen
Marja-Leena Kortelainen
Gabrielle Boucher
Caroline Lagacé
Anna Moes
XiaoQing Zhao
Frank Kolodgie
Fernando Rivadeneira
Albert Hofman
Jacqueline C M Witteman
André G Uitterlinden
Roos F Marsman
Raha Pazoki
Abdennasser Bardai
Rudolph W Koster
Abbas Dehghan
Shih-Jen Hwang
Pallav Bhatnagar
Wendy Post
Gina Hilton
Ronald J Prineas
Man Li
Anna Köttgen
Georg Ehret
Eric Boerwinkle
Josef Coresh
W H Linda Kao
Bruce M Psaty
Gordon F Tomaselli
Nona Sotoodehnia
David S Siscovick
Greg L Burke
Eduardo Marbán
Peter M Spooner
L Adrienne Cupples
Jonathan Jui
Karen Gunson
Y Antero Kesäniemi
Arthur A M Wilde
Jean-Claude Tardif
Christopher J O'Donnell
Connie R Bezzina
Renu Virmani
Bruno H C H Stricker
Hanno L Tan
Christine M Albert
Aravinda Chakravarti
John D Rioux
Heikki V Huikuri
Sumeet S Chugh
Identification of a sudden cardiac death susceptibility locus at 2q24.2 through genome-wide association in European ancestry individuals.
PLoS Genetics
title Identification of a sudden cardiac death susceptibility locus at 2q24.2 through genome-wide association in European ancestry individuals.
title_full Identification of a sudden cardiac death susceptibility locus at 2q24.2 through genome-wide association in European ancestry individuals.
title_fullStr Identification of a sudden cardiac death susceptibility locus at 2q24.2 through genome-wide association in European ancestry individuals.
title_full_unstemmed Identification of a sudden cardiac death susceptibility locus at 2q24.2 through genome-wide association in European ancestry individuals.
title_short Identification of a sudden cardiac death susceptibility locus at 2q24.2 through genome-wide association in European ancestry individuals.
title_sort identification of a sudden cardiac death susceptibility locus at 2q24 2 through genome wide association in european ancestry individuals
url https://journals.plos.org/plosgenetics/article/file?id=10.1371/journal.pgen.1002158&type=printable
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