Mediastinal Tracheostoma for Treatment of Tracheostenosis after Tracheostomy in a Patient with Mucopolysaccharidosis-Induced Tracheomalacia

Background. Treatment of tracheostenosis after tracheostomy in pediatric patients is often difficult. Mucopolysaccharidosis is a lysosomal storage disease that may induce obstruction of the airways. Case Presentation. A 16-year-old male patient underwent long-term follow-up after postnatal diagnosis...

Full description

Saved in:
Bibliographic Details
Main Authors: Yasuhiro Chikaishi, Kenichi Kobayashi, Shuichi Shinohara, Akihiro Taira, Yusuke Nabe, Shinji Shinohara, Taiji Kuwata, Masaru Takenaka, Soichi Oka, Ayako Hirai, Kazue Yoneda, Koji Kuroda, Naoko Imanishi, Yoshinobu Ichiki, Fumihiro Tanaka
Format: Article
Language:English
Published: Wiley 2017-01-01
Series:Case Reports in Surgery
Online Access:http://dx.doi.org/10.1155/2017/2312415
Tags: Add Tag
No Tags, Be the first to tag this record!
_version_ 1832545854975639552
author Yasuhiro Chikaishi
Kenichi Kobayashi
Shuichi Shinohara
Akihiro Taira
Yusuke Nabe
Shinji Shinohara
Taiji Kuwata
Masaru Takenaka
Soichi Oka
Ayako Hirai
Kazue Yoneda
Koji Kuroda
Naoko Imanishi
Yoshinobu Ichiki
Fumihiro Tanaka
author_facet Yasuhiro Chikaishi
Kenichi Kobayashi
Shuichi Shinohara
Akihiro Taira
Yusuke Nabe
Shinji Shinohara
Taiji Kuwata
Masaru Takenaka
Soichi Oka
Ayako Hirai
Kazue Yoneda
Koji Kuroda
Naoko Imanishi
Yoshinobu Ichiki
Fumihiro Tanaka
author_sort Yasuhiro Chikaishi
collection DOAJ
description Background. Treatment of tracheostenosis after tracheostomy in pediatric patients is often difficult. Mucopolysaccharidosis is a lysosomal storage disease that may induce obstruction of the airways. Case Presentation. A 16-year-old male patient underwent long-term follow-up after postnatal diagnosis of type II mucopolysaccharidosis. At 11 years of age, tracheostomy was performed for mucopolysaccharidosis-induced laryngeal stenosis. One week prior to presentation, he was admitted to another hospital on an emergency basis for major dyspnea. He was diagnosed with tracheostenosis caused by granulation. The patient was then referred to our institution. The peripheral view of his airway was difficult because of mucopolysaccharidosis-induced tracheomalacia. For airway management, a mediastinal tracheostoma was created with extracorporeal membrane oxygenation. To maintain the blood flow, the skin incision for the mediastinal tracheal hole was sharply cut without an electrotome. The postoperative course was uneventful, and the patient was weaned from the ventilator on postoperative day 19. He was discharged 1.5 months postoperatively. Although he was referred to another institution because of respiratory failure caused by his primary disease 6 months postoperatively, his airway management remained successful for 1.5 years postoperatively. Conclusion. Mediastinal tracheostomy was useful for treatment of tracheostenosis caused by granulation tissue formation after a tracheostomy.
format Article
id doaj-art-648d61ee67794b069343c7e02d36bba1
institution Kabale University
issn 2090-6900
2090-6919
language English
publishDate 2017-01-01
publisher Wiley
record_format Article
series Case Reports in Surgery
spelling doaj-art-648d61ee67794b069343c7e02d36bba12025-02-03T07:24:35ZengWileyCase Reports in Surgery2090-69002090-69192017-01-01201710.1155/2017/23124152312415Mediastinal Tracheostoma for Treatment of Tracheostenosis after Tracheostomy in a Patient with Mucopolysaccharidosis-Induced TracheomalaciaYasuhiro Chikaishi0Kenichi Kobayashi1Shuichi Shinohara2Akihiro Taira3Yusuke Nabe4Shinji Shinohara5Taiji Kuwata6Masaru Takenaka7Soichi Oka8Ayako Hirai9Kazue Yoneda10Koji Kuroda11Naoko Imanishi12Yoshinobu Ichiki13Fumihiro Tanaka14Second Department of Surgery, School of Medicine, University of Occupational and Environmental Health, 1-1 Iseigaoka, Yahatanishi-ku, Kitakyushu 807-8555, JapanSecond Department of Surgery, School of Medicine, University of Occupational and Environmental Health, 1-1 Iseigaoka, Yahatanishi-ku, Kitakyushu 807-8555, JapanSecond Department of Surgery, School of Medicine, University of Occupational and Environmental Health, 1-1 Iseigaoka, Yahatanishi-ku, Kitakyushu 807-8555, JapanSecond Department of Surgery, School of Medicine, University of Occupational and Environmental Health, 1-1 Iseigaoka, Yahatanishi-ku, Kitakyushu 807-8555, JapanSecond Department of Surgery, School of Medicine, University of Occupational and Environmental Health, 1-1 Iseigaoka, Yahatanishi-ku, Kitakyushu 807-8555, JapanSecond Department of Surgery, School of Medicine, University of Occupational and Environmental Health, 1-1 Iseigaoka, Yahatanishi-ku, Kitakyushu 807-8555, JapanSecond Department of Surgery, School of Medicine, University of Occupational and Environmental Health, 1-1 Iseigaoka, Yahatanishi-ku, Kitakyushu 807-8555, JapanSecond Department of Surgery, School of Medicine, University of Occupational and Environmental Health, 1-1 Iseigaoka, Yahatanishi-ku, Kitakyushu 807-8555, JapanSecond Department of Surgery, School of Medicine, University of Occupational and Environmental Health, 1-1 Iseigaoka, Yahatanishi-ku, Kitakyushu 807-8555, JapanSecond Department of Surgery, School of Medicine, University of Occupational and Environmental Health, 1-1 Iseigaoka, Yahatanishi-ku, Kitakyushu 807-8555, JapanSecond Department of Surgery, School of Medicine, University of Occupational and Environmental Health, 1-1 Iseigaoka, Yahatanishi-ku, Kitakyushu 807-8555, JapanSecond Department of Surgery, School of Medicine, University of Occupational and Environmental Health, 1-1 Iseigaoka, Yahatanishi-ku, Kitakyushu 807-8555, JapanSecond Department of Surgery, School of Medicine, University of Occupational and Environmental Health, 1-1 Iseigaoka, Yahatanishi-ku, Kitakyushu 807-8555, JapanSecond Department of Surgery, School of Medicine, University of Occupational and Environmental Health, 1-1 Iseigaoka, Yahatanishi-ku, Kitakyushu 807-8555, JapanSecond Department of Surgery, School of Medicine, University of Occupational and Environmental Health, 1-1 Iseigaoka, Yahatanishi-ku, Kitakyushu 807-8555, JapanBackground. Treatment of tracheostenosis after tracheostomy in pediatric patients is often difficult. Mucopolysaccharidosis is a lysosomal storage disease that may induce obstruction of the airways. Case Presentation. A 16-year-old male patient underwent long-term follow-up after postnatal diagnosis of type II mucopolysaccharidosis. At 11 years of age, tracheostomy was performed for mucopolysaccharidosis-induced laryngeal stenosis. One week prior to presentation, he was admitted to another hospital on an emergency basis for major dyspnea. He was diagnosed with tracheostenosis caused by granulation. The patient was then referred to our institution. The peripheral view of his airway was difficult because of mucopolysaccharidosis-induced tracheomalacia. For airway management, a mediastinal tracheostoma was created with extracorporeal membrane oxygenation. To maintain the blood flow, the skin incision for the mediastinal tracheal hole was sharply cut without an electrotome. The postoperative course was uneventful, and the patient was weaned from the ventilator on postoperative day 19. He was discharged 1.5 months postoperatively. Although he was referred to another institution because of respiratory failure caused by his primary disease 6 months postoperatively, his airway management remained successful for 1.5 years postoperatively. Conclusion. Mediastinal tracheostomy was useful for treatment of tracheostenosis caused by granulation tissue formation after a tracheostomy.http://dx.doi.org/10.1155/2017/2312415
spellingShingle Yasuhiro Chikaishi
Kenichi Kobayashi
Shuichi Shinohara
Akihiro Taira
Yusuke Nabe
Shinji Shinohara
Taiji Kuwata
Masaru Takenaka
Soichi Oka
Ayako Hirai
Kazue Yoneda
Koji Kuroda
Naoko Imanishi
Yoshinobu Ichiki
Fumihiro Tanaka
Mediastinal Tracheostoma for Treatment of Tracheostenosis after Tracheostomy in a Patient with Mucopolysaccharidosis-Induced Tracheomalacia
Case Reports in Surgery
title Mediastinal Tracheostoma for Treatment of Tracheostenosis after Tracheostomy in a Patient with Mucopolysaccharidosis-Induced Tracheomalacia
title_full Mediastinal Tracheostoma for Treatment of Tracheostenosis after Tracheostomy in a Patient with Mucopolysaccharidosis-Induced Tracheomalacia
title_fullStr Mediastinal Tracheostoma for Treatment of Tracheostenosis after Tracheostomy in a Patient with Mucopolysaccharidosis-Induced Tracheomalacia
title_full_unstemmed Mediastinal Tracheostoma for Treatment of Tracheostenosis after Tracheostomy in a Patient with Mucopolysaccharidosis-Induced Tracheomalacia
title_short Mediastinal Tracheostoma for Treatment of Tracheostenosis after Tracheostomy in a Patient with Mucopolysaccharidosis-Induced Tracheomalacia
title_sort mediastinal tracheostoma for treatment of tracheostenosis after tracheostomy in a patient with mucopolysaccharidosis induced tracheomalacia
url http://dx.doi.org/10.1155/2017/2312415
work_keys_str_mv AT yasuhirochikaishi mediastinaltracheostomafortreatmentoftracheostenosisaftertracheostomyinapatientwithmucopolysaccharidosisinducedtracheomalacia
AT kenichikobayashi mediastinaltracheostomafortreatmentoftracheostenosisaftertracheostomyinapatientwithmucopolysaccharidosisinducedtracheomalacia
AT shuichishinohara mediastinaltracheostomafortreatmentoftracheostenosisaftertracheostomyinapatientwithmucopolysaccharidosisinducedtracheomalacia
AT akihirotaira mediastinaltracheostomafortreatmentoftracheostenosisaftertracheostomyinapatientwithmucopolysaccharidosisinducedtracheomalacia
AT yusukenabe mediastinaltracheostomafortreatmentoftracheostenosisaftertracheostomyinapatientwithmucopolysaccharidosisinducedtracheomalacia
AT shinjishinohara mediastinaltracheostomafortreatmentoftracheostenosisaftertracheostomyinapatientwithmucopolysaccharidosisinducedtracheomalacia
AT taijikuwata mediastinaltracheostomafortreatmentoftracheostenosisaftertracheostomyinapatientwithmucopolysaccharidosisinducedtracheomalacia
AT masarutakenaka mediastinaltracheostomafortreatmentoftracheostenosisaftertracheostomyinapatientwithmucopolysaccharidosisinducedtracheomalacia
AT soichioka mediastinaltracheostomafortreatmentoftracheostenosisaftertracheostomyinapatientwithmucopolysaccharidosisinducedtracheomalacia
AT ayakohirai mediastinaltracheostomafortreatmentoftracheostenosisaftertracheostomyinapatientwithmucopolysaccharidosisinducedtracheomalacia
AT kazueyoneda mediastinaltracheostomafortreatmentoftracheostenosisaftertracheostomyinapatientwithmucopolysaccharidosisinducedtracheomalacia
AT kojikuroda mediastinaltracheostomafortreatmentoftracheostenosisaftertracheostomyinapatientwithmucopolysaccharidosisinducedtracheomalacia
AT naokoimanishi mediastinaltracheostomafortreatmentoftracheostenosisaftertracheostomyinapatientwithmucopolysaccharidosisinducedtracheomalacia
AT yoshinobuichiki mediastinaltracheostomafortreatmentoftracheostenosisaftertracheostomyinapatientwithmucopolysaccharidosisinducedtracheomalacia
AT fumihirotanaka mediastinaltracheostomafortreatmentoftracheostenosisaftertracheostomyinapatientwithmucopolysaccharidosisinducedtracheomalacia