Unmasking inborn errors of immunity: identifying the red flags of immune dysregulation

Inborn errors of immunity (IEI) are rare diseases that affect the immune system. According to the latest International Union of Immunological Societies (IUIS) classification, 485 different IEI have been identified. Even if increased susceptibility to infections is the best-known symptom, IEI are no...

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Main Authors: Manuela Cortesi, Laura Dotta, Marco Cattalini, Vassilios Lougaris, Annarosa Soresina, Raffaele Badolato
Format: Article
Language:English
Published: Frontiers Media S.A. 2024-12-01
Series:Frontiers in Immunology
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Online Access:https://www.frontiersin.org/articles/10.3389/fimmu.2024.1497921/full
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author Manuela Cortesi
Laura Dotta
Marco Cattalini
Vassilios Lougaris
Annarosa Soresina
Raffaele Badolato
author_facet Manuela Cortesi
Laura Dotta
Marco Cattalini
Vassilios Lougaris
Annarosa Soresina
Raffaele Badolato
author_sort Manuela Cortesi
collection DOAJ
description Inborn errors of immunity (IEI) are rare diseases that affect the immune system. According to the latest International Union of Immunological Societies (IUIS) classification, 485 different IEI have been identified. Even if increased susceptibility to infections is the best-known symptom, IEI are no longer defined by the higher likelihood of infections alone. Immune dysregulation with autoimmune disease and hyperinflammation, lymphoproliferation, and malignancy are common manifestations and could be the only symptoms of IEI that must be recognized. An exclusive focus on infection-centered warning signs would miss around 25% of patients with IEI who initially present with other manifestations. Timely and appropriate diagnosis and treatment are essential to enhance the quality of life (QoL) and, in some cases, survival, as patients are susceptible to life-threatening infections or autoimmunity. In addition, the advantage of early diagnosis in IEI with immune dysregulation (i.e. CTLA4 deficiency, LRBA deficiency, NF-kB1/NF-kB2 deficiency, activated phosphoinositide 3-kinase delta syndrome -APDS-) is the initiation of targeted therapies with precise re-balancing of the dysregulated immune pathways (i.e., biologicals, selective inhibitors) or definitive therapy (i.e., HSCT).
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spelling doaj-art-4bbe48f864e84d43a4b081162cc063e12025-08-20T02:52:20ZengFrontiers Media S.A.Frontiers in Immunology1664-32242024-12-011510.3389/fimmu.2024.14979211497921Unmasking inborn errors of immunity: identifying the red flags of immune dysregulationManuela CortesiLaura DottaMarco CattaliniVassilios LougarisAnnarosa SoresinaRaffaele BadolatoInborn errors of immunity (IEI) are rare diseases that affect the immune system. According to the latest International Union of Immunological Societies (IUIS) classification, 485 different IEI have been identified. Even if increased susceptibility to infections is the best-known symptom, IEI are no longer defined by the higher likelihood of infections alone. Immune dysregulation with autoimmune disease and hyperinflammation, lymphoproliferation, and malignancy are common manifestations and could be the only symptoms of IEI that must be recognized. An exclusive focus on infection-centered warning signs would miss around 25% of patients with IEI who initially present with other manifestations. Timely and appropriate diagnosis and treatment are essential to enhance the quality of life (QoL) and, in some cases, survival, as patients are susceptible to life-threatening infections or autoimmunity. In addition, the advantage of early diagnosis in IEI with immune dysregulation (i.e. CTLA4 deficiency, LRBA deficiency, NF-kB1/NF-kB2 deficiency, activated phosphoinositide 3-kinase delta syndrome -APDS-) is the initiation of targeted therapies with precise re-balancing of the dysregulated immune pathways (i.e., biologicals, selective inhibitors) or definitive therapy (i.e., HSCT).https://www.frontiersin.org/articles/10.3389/fimmu.2024.1497921/fullinborn errors of immunityimmune dysregulationautoimmunityAPDswarning signs
spellingShingle Manuela Cortesi
Laura Dotta
Marco Cattalini
Vassilios Lougaris
Annarosa Soresina
Raffaele Badolato
Unmasking inborn errors of immunity: identifying the red flags of immune dysregulation
Frontiers in Immunology
inborn errors of immunity
immune dysregulation
autoimmunity
APDs
warning signs
title Unmasking inborn errors of immunity: identifying the red flags of immune dysregulation
title_full Unmasking inborn errors of immunity: identifying the red flags of immune dysregulation
title_fullStr Unmasking inborn errors of immunity: identifying the red flags of immune dysregulation
title_full_unstemmed Unmasking inborn errors of immunity: identifying the red flags of immune dysregulation
title_short Unmasking inborn errors of immunity: identifying the red flags of immune dysregulation
title_sort unmasking inborn errors of immunity identifying the red flags of immune dysregulation
topic inborn errors of immunity
immune dysregulation
autoimmunity
APDs
warning signs
url https://www.frontiersin.org/articles/10.3389/fimmu.2024.1497921/full
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