Congenital H-type recto-vaginal fistula with normal anus: a case report

Introduction: Congenital H-type fistula is a rare anomaly characterized by a recto-urogenital connection, with the external anal opening potentially positioned normally or ectopically. This type of fistula represents only 0.1 % of all anorectal malformations in Africa. Case description: A 6-week-old...

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Main Authors: Samuel Kefiyalew Kelbessa, Berhanu Nigusse Bikila, Amanuel Mesfin Oljira
Format: Article
Language:English
Published: Elsevier 2025-09-01
Series:Journal of Pediatric Surgery Case Reports
Online Access:http://www.sciencedirect.com/science/article/pii/S2213576625000995
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author Samuel Kefiyalew Kelbessa
Berhanu Nigusse Bikila
Amanuel Mesfin Oljira
author_facet Samuel Kefiyalew Kelbessa
Berhanu Nigusse Bikila
Amanuel Mesfin Oljira
author_sort Samuel Kefiyalew Kelbessa
collection DOAJ
description Introduction: Congenital H-type fistula is a rare anomaly characterized by a recto-urogenital connection, with the external anal opening potentially positioned normally or ectopically. This type of fistula represents only 0.1 % of all anorectal malformations in Africa. Case description: A 6-week-old female infant was referred to our clinic after feces were noted coming from both the anus and the vaginal vestibulum. Examination under anesthesia revealed a non-stenotic anus and a fistulous opening on the anterior rectal wall, 1.5 cm above the dentate line. Preoperative VACTERL screening was normal. The infant received two doses of a cleansing enema and intravenous preoperative antibiotics (ceftriaxone and metronidazole). Under general anesthesia, a loop proximal sigmoid colostomy was performed. The infant was positioned prone for a transanal anterior rectal pull-through. A Swenson-like dissection was conducted on the anterior rectal wall for 4 cm, leaving the posterior wall intact. The vaginal opening was repaired using interrupted sutures. The left ischiorectal fat pad was harvested and placed between the repaired vaginal wall and the anterior rectal wall. The full-thickness rectal wall was then pulled over and anastomosed to the anus. The patient was discharged home after three days. The colostomy was closed three months later. One year after the operation she has no signs of fistula recurrence. Conclusion: A transanal anterior rectal pull-through with protective colostomy seems to be an effective option for the management of H-type congenital rectovaginal fistulas in neonates and infants.
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spelling doaj-art-43d76e204aeb44309d9d357ff8ef82f82025-08-20T02:47:24ZengElsevierJournal of Pediatric Surgery Case Reports2213-57662025-09-0112010305410.1016/j.epsc.2025.103054Congenital H-type recto-vaginal fistula with normal anus: a case reportSamuel Kefiyalew Kelbessa0Berhanu Nigusse Bikila1Amanuel Mesfin Oljira2Corresponding author. Pediatric Surgery Division, Ambo University Referral Hospital, Ambo University, Ambo, Ethiopia.; Department of Surgery, Ambo University Referral Hospital, Ambo University, Ambo, EthiopiaDepartment of Surgery, Ambo University Referral Hospital, Ambo University, Ambo, EthiopiaDepartment of Surgery, Ambo University Referral Hospital, Ambo University, Ambo, EthiopiaIntroduction: Congenital H-type fistula is a rare anomaly characterized by a recto-urogenital connection, with the external anal opening potentially positioned normally or ectopically. This type of fistula represents only 0.1 % of all anorectal malformations in Africa. Case description: A 6-week-old female infant was referred to our clinic after feces were noted coming from both the anus and the vaginal vestibulum. Examination under anesthesia revealed a non-stenotic anus and a fistulous opening on the anterior rectal wall, 1.5 cm above the dentate line. Preoperative VACTERL screening was normal. The infant received two doses of a cleansing enema and intravenous preoperative antibiotics (ceftriaxone and metronidazole). Under general anesthesia, a loop proximal sigmoid colostomy was performed. The infant was positioned prone for a transanal anterior rectal pull-through. A Swenson-like dissection was conducted on the anterior rectal wall for 4 cm, leaving the posterior wall intact. The vaginal opening was repaired using interrupted sutures. The left ischiorectal fat pad was harvested and placed between the repaired vaginal wall and the anterior rectal wall. The full-thickness rectal wall was then pulled over and anastomosed to the anus. The patient was discharged home after three days. The colostomy was closed three months later. One year after the operation she has no signs of fistula recurrence. Conclusion: A transanal anterior rectal pull-through with protective colostomy seems to be an effective option for the management of H-type congenital rectovaginal fistulas in neonates and infants.http://www.sciencedirect.com/science/article/pii/S2213576625000995
spellingShingle Samuel Kefiyalew Kelbessa
Berhanu Nigusse Bikila
Amanuel Mesfin Oljira
Congenital H-type recto-vaginal fistula with normal anus: a case report
Journal of Pediatric Surgery Case Reports
title Congenital H-type recto-vaginal fistula with normal anus: a case report
title_full Congenital H-type recto-vaginal fistula with normal anus: a case report
title_fullStr Congenital H-type recto-vaginal fistula with normal anus: a case report
title_full_unstemmed Congenital H-type recto-vaginal fistula with normal anus: a case report
title_short Congenital H-type recto-vaginal fistula with normal anus: a case report
title_sort congenital h type recto vaginal fistula with normal anus a case report
url http://www.sciencedirect.com/science/article/pii/S2213576625000995
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