Ipsilateral Hip Dysplasia in Patients with Sacral Hemiagenesis: A Report of Two Cases

Sacral agenesis (SA) is a rare condition consisting of the imperfect development of any part of the sacrum. This paper describes two cases of the rare cooccurrence of ipsilateral SA and developmental dysplasia of the hip (DDH) and analyzes possible contributory factors for SA and DDH. Each of a 16-y...

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Main Authors: Tadatsugu Morimoto, Motoki Sonohata, Masaaki Mawatari
Format: Article
Language:English
Published: Wiley 2015-01-01
Series:Case Reports in Orthopedics
Online Access:http://dx.doi.org/10.1155/2015/854151
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author Tadatsugu Morimoto
Motoki Sonohata
Masaaki Mawatari
author_facet Tadatsugu Morimoto
Motoki Sonohata
Masaaki Mawatari
author_sort Tadatsugu Morimoto
collection DOAJ
description Sacral agenesis (SA) is a rare condition consisting of the imperfect development of any part of the sacrum. This paper describes two cases of the rare cooccurrence of ipsilateral SA and developmental dysplasia of the hip (DDH) and analyzes possible contributory factors for SA and DDH. Each of a 16-year-old female and 13-year-old female visited our hospital for left hip pain and limping. The findings of physical examinations showed a lower limb length discrepancy (left side) in both cases, as well as left hip pain without limitations of the range of motion or neurological deficits. Initial radiographs demonstrated left subluxation of the left hip with associated acetabular dysplasia and partial left sacral agenesis. MRI revealed a tethering cord with a fatty filum terminale, and periacetabular osteotomy combined with allogeneic bone grafting was performed. After the surgery, the patients experienced no further pain, with no leg length discrepancy and were able to walk without a limp, being neurologically normal with a normal left hip range of motion. The cooccurrence of SA and DDH suggests a plausible hypothesis to explain the embryogenic relationship between malformation of the sacrum and hip.
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spelling doaj-art-1559b2aa332348408f3e93a077c2408b2025-02-03T06:08:09ZengWileyCase Reports in Orthopedics2090-67492090-67572015-01-01201510.1155/2015/854151854151Ipsilateral Hip Dysplasia in Patients with Sacral Hemiagenesis: A Report of Two CasesTadatsugu Morimoto0Motoki Sonohata1Masaaki Mawatari2Department of Orthopaedic Surgery, Faculty of Medicine, Saga University, 5-1-1 Nabeshima, Saga 849-8501, JapanDepartment of Orthopaedic Surgery, Faculty of Medicine, Saga University, 5-1-1 Nabeshima, Saga 849-8501, JapanDepartment of Orthopaedic Surgery, Faculty of Medicine, Saga University, 5-1-1 Nabeshima, Saga 849-8501, JapanSacral agenesis (SA) is a rare condition consisting of the imperfect development of any part of the sacrum. This paper describes two cases of the rare cooccurrence of ipsilateral SA and developmental dysplasia of the hip (DDH) and analyzes possible contributory factors for SA and DDH. Each of a 16-year-old female and 13-year-old female visited our hospital for left hip pain and limping. The findings of physical examinations showed a lower limb length discrepancy (left side) in both cases, as well as left hip pain without limitations of the range of motion or neurological deficits. Initial radiographs demonstrated left subluxation of the left hip with associated acetabular dysplasia and partial left sacral agenesis. MRI revealed a tethering cord with a fatty filum terminale, and periacetabular osteotomy combined with allogeneic bone grafting was performed. After the surgery, the patients experienced no further pain, with no leg length discrepancy and were able to walk without a limp, being neurologically normal with a normal left hip range of motion. The cooccurrence of SA and DDH suggests a plausible hypothesis to explain the embryogenic relationship between malformation of the sacrum and hip.http://dx.doi.org/10.1155/2015/854151
spellingShingle Tadatsugu Morimoto
Motoki Sonohata
Masaaki Mawatari
Ipsilateral Hip Dysplasia in Patients with Sacral Hemiagenesis: A Report of Two Cases
Case Reports in Orthopedics
title Ipsilateral Hip Dysplasia in Patients with Sacral Hemiagenesis: A Report of Two Cases
title_full Ipsilateral Hip Dysplasia in Patients with Sacral Hemiagenesis: A Report of Two Cases
title_fullStr Ipsilateral Hip Dysplasia in Patients with Sacral Hemiagenesis: A Report of Two Cases
title_full_unstemmed Ipsilateral Hip Dysplasia in Patients with Sacral Hemiagenesis: A Report of Two Cases
title_short Ipsilateral Hip Dysplasia in Patients with Sacral Hemiagenesis: A Report of Two Cases
title_sort ipsilateral hip dysplasia in patients with sacral hemiagenesis a report of two cases
url http://dx.doi.org/10.1155/2015/854151
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AT masaakimawatari ipsilateralhipdysplasiainpatientswithsacralhemiagenesisareportoftwocases