Ectopia Cordis with Omphalocele in First Trimester Pregnancy: A Case Report of Incomplete Type of Pentalogy of Cantrell

Ectopia Cordis (EC) is a rare congenital malformation in which the heart is located partially or totally outside the thoracic cavity. It results from the failure of migration of the lateral mesoderm into the midline. The four main ectopic positions are cervical, thoracic, thoracoabdominal and abdomi...

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Main Authors: Arumulla Mithilesh, Hira Muhammed, Yugandhar Samireddypalle, Nanditha Jangamreddy
Format: Article
Language:English
Published: JCDR Research and Publications Pvt. Ltd. 2024-09-01
Series:International Journal of Anatomy Radiology and Surgery
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Online Access:https://www.ijars.net/articles/PDF/3017/71423_CE[Ra1]_F(SHU)_QC(PS_SHU)_PF1(JY_SHU)_redo_PFA_NC(SHU)_PN(SHU).pdf
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author Arumulla Mithilesh
Hira Muhammed
Yugandhar Samireddypalle
Nanditha Jangamreddy
author_facet Arumulla Mithilesh
Hira Muhammed
Yugandhar Samireddypalle
Nanditha Jangamreddy
author_sort Arumulla Mithilesh
collection DOAJ
description Ectopia Cordis (EC) is a rare congenital malformation in which the heart is located partially or totally outside the thoracic cavity. It results from the failure of migration of the lateral mesoderm into the midline. The four main ectopic positions are cervical, thoracic, thoracoabdominal and abdominal. EC can manifest as an isolated deformity or as part of a broader group of ventral body wall defects affecting the abdomen, thorax, or both. Pentalogy of Cantrell is a well known association that comprises EC, omphalocele (typically supraumbilical), congenital diaphragmatic hernia, sternal cleft and congenital heart disease. A 27-year-old primigravida came for a routine antenatal ultrasound at 13 weeks of gestation. There was no family history of congenital anomalies, genetic abnormalities, or exposure to teratogenic agents. The ultrasound showed a single foetus corresponding to 13 weeks of gestation with an anterior thoracic defect and an extrathoracic heart, along with partial herniation of the liver near the midline in the epigastric region. These findings were confirmed by foetal Magnetic Resonance Imaging (MRI). An unfavourable prognosis for the foetus was explained to the parents, and medical termination of pregnancy was performed. Therefore, prenatal ultrasonographic diagnosis of EC should be followed by a thorough search for associated defects, as the prognosis may vary.
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issn 2277-8543
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language English
publishDate 2024-09-01
publisher JCDR Research and Publications Pvt. Ltd.
record_format Article
series International Journal of Anatomy Radiology and Surgery
spelling doaj-art-096599f2ab8a4b45b3d96bb0d88cce2b2025-08-20T02:10:53ZengJCDR Research and Publications Pvt. Ltd.International Journal of Anatomy Radiology and Surgery2277-85432455-68742024-09-011305111310.7860/IJARS/2024/71423.3017Ectopia Cordis with Omphalocele in First Trimester Pregnancy: A Case Report of Incomplete Type of Pentalogy of CantrellArumulla Mithilesh0Hira Muhammed1Yugandhar Samireddypalle2Nanditha Jangamreddy3Assistant Professor, Department of Radiodiagnosis, AIIMS Mangalagiri, Andhra Pradesh, India.Junior Resident, Department of Radiodiagnosis, AIIMS Mangalagiri, Andhra Pradesh, India.Assistant Professor, Department of Radiodiagnosis, AIIMS Mangalagiri, Andhra Pradesh, India.Senior Resident, Department of Obstetrics and Gynaecology, AIIMS Mangalagiri, Andhra Pradesh, India.Ectopia Cordis (EC) is a rare congenital malformation in which the heart is located partially or totally outside the thoracic cavity. It results from the failure of migration of the lateral mesoderm into the midline. The four main ectopic positions are cervical, thoracic, thoracoabdominal and abdominal. EC can manifest as an isolated deformity or as part of a broader group of ventral body wall defects affecting the abdomen, thorax, or both. Pentalogy of Cantrell is a well known association that comprises EC, omphalocele (typically supraumbilical), congenital diaphragmatic hernia, sternal cleft and congenital heart disease. A 27-year-old primigravida came for a routine antenatal ultrasound at 13 weeks of gestation. There was no family history of congenital anomalies, genetic abnormalities, or exposure to teratogenic agents. The ultrasound showed a single foetus corresponding to 13 weeks of gestation with an anterior thoracic defect and an extrathoracic heart, along with partial herniation of the liver near the midline in the epigastric region. These findings were confirmed by foetal Magnetic Resonance Imaging (MRI). An unfavourable prognosis for the foetus was explained to the parents, and medical termination of pregnancy was performed. Therefore, prenatal ultrasonographic diagnosis of EC should be followed by a thorough search for associated defects, as the prognosis may vary.https://www.ijars.net/articles/PDF/3017/71423_CE[Ra1]_F(SHU)_QC(PS_SHU)_PF1(JY_SHU)_redo_PFA_NC(SHU)_PN(SHU).pdfantenatal ultrasonographyanterior abdominal wall defectscongenital anomaliesfoetus
spellingShingle Arumulla Mithilesh
Hira Muhammed
Yugandhar Samireddypalle
Nanditha Jangamreddy
Ectopia Cordis with Omphalocele in First Trimester Pregnancy: A Case Report of Incomplete Type of Pentalogy of Cantrell
International Journal of Anatomy Radiology and Surgery
antenatal ultrasonography
anterior abdominal wall defects
congenital anomalies
foetus
title Ectopia Cordis with Omphalocele in First Trimester Pregnancy: A Case Report of Incomplete Type of Pentalogy of Cantrell
title_full Ectopia Cordis with Omphalocele in First Trimester Pregnancy: A Case Report of Incomplete Type of Pentalogy of Cantrell
title_fullStr Ectopia Cordis with Omphalocele in First Trimester Pregnancy: A Case Report of Incomplete Type of Pentalogy of Cantrell
title_full_unstemmed Ectopia Cordis with Omphalocele in First Trimester Pregnancy: A Case Report of Incomplete Type of Pentalogy of Cantrell
title_short Ectopia Cordis with Omphalocele in First Trimester Pregnancy: A Case Report of Incomplete Type of Pentalogy of Cantrell
title_sort ectopia cordis with omphalocele in first trimester pregnancy a case report of incomplete type of pentalogy of cantrell
topic antenatal ultrasonography
anterior abdominal wall defects
congenital anomalies
foetus
url https://www.ijars.net/articles/PDF/3017/71423_CE[Ra1]_F(SHU)_QC(PS_SHU)_PF1(JY_SHU)_redo_PFA_NC(SHU)_PN(SHU).pdf
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